Boeras Debrah I, Granic Antoneta, Padmanabhan Jaya, Crespo Nichole C, Rojiani Amyn M, Potter Huntington
Department of Molecular Medicine and Suncoast Gerontology Center, University of South Florida, College of Medicine, Tampa, FL 33612, USA.
Neurobiol Aging. 2008 Mar;29(3):319-28. doi: 10.1016/j.neurobiolaging.2006.10.027. Epub 2006 Dec 13.
Mutations in the presenilin 1 gene cause most early onset familial Alzheimer's disease (FAD). Here, we report that a defect in the cell cycle - improper chromosome segregation - can be caused by abnormal presenilin function and therefore may contribute to AD pathogenesis. Specifically we find that either over-expression or FAD mutation in presenilin 1 (M146L and M146V) leads to chromosome missegregation and aneuploidy in vivo and in vitro: (1) Up to 20% of lymphocytes and neurons of FAD-PS-1 transgenic and knocking mice are aneuploid by metaphase chromosome analysis and in situ hybridization. (2) Transiently transfected human cells over-expressing normal or mutant PS-1 develop similar aneuploidy within 48 h, including trisomy 21. (3) Mitotic spindles in the PS-1 transfected cells contain abnormal microtubule arrays and lagging chromosomes. Several mechanisms by which chromosome missegregation induced by presenilin may contribute to Alzheimer's disease are discussed.
早老素1基因的突变会引发大多数早发性家族性阿尔茨海默病(FAD)。在此,我们报告细胞周期缺陷——染色体分离异常——可由早老素功能异常引起,因此可能与阿尔茨海默病的发病机制有关。具体而言,我们发现早老素1的过表达或FAD突变(M146L和M146V)在体内和体外均会导致染色体错分离和非整倍体:(1)通过中期染色体分析和原位杂交,FAD-PS-1转基因和敲除小鼠中高达20%的淋巴细胞和神经元为非整倍体。(2)瞬时转染过表达正常或突变型PS-1的人类细胞在48小时内会出现类似的非整倍体,包括21三体。(3)PS-1转染细胞中的有丝分裂纺锤体含有异常的微管阵列和滞后染色体。文中讨论了早老素诱导的染色体错分离可能导致阿尔茨海默病的几种机制。