Fernández M, Pacheco M, Garaizar C, Prats J M
Departamento de Pediatría, Hospital de Cruces, Baracaldo, Vizcaya.
Neurologia. 1991 Aug-Sep;6(7):259-62.
A case of congenital atonic-sclerotic muscular dystrophy is described, with a combination of proximal joint rigidity and distal hypotonia and hyperextensibility, besides torticollis and kyphoscoliosis. These severe congenital defects usually prevent walking and are followed by chronic respiratory insufficiency, with a fatal outcome in the long term. An autosomal recessive type of heredity is implied. There is not sensory or intellectual impairment, therefore it can be distinguished from other congenital muscular dystrophies, that usually have CNS abnormalities associated.
本文描述了一例先天性张力缺乏-硬化性肌营养不良病例,除斜颈和脊柱侧凸外,还伴有近端关节僵硬以及远端肌张力减退和关节过度伸展。这些严重的先天性缺陷通常会导致无法行走,并继而引发慢性呼吸功能不全,长期来看会导致致命后果。提示为常染色体隐性遗传类型。不存在感觉或智力障碍,因此可与其他通常伴有中枢神经系统异常的先天性肌营养不良相鉴别。