Pandhi Deepika, Khanna Deepshikha, Singal Archana, Madhu Sri Venkata
Department of Dermatology and STD, University College of Medical Sciences, and Guru Teg Bahadur Hospital, Delhi, 110095, India.
Arch Dermatol Res. 2007 Nov;299(9):457-60. doi: 10.1007/s00403-007-0783-4. Epub 2007 Sep 6.
A 15-year-old male presented with ichthyosis since infancy with panhypopituitarism, short stature and knock-knees, delayed puberty, high scrotal retractile testes, mental retardation and corneal opacities. He developed recurrent tinea capitis and tinea corporis. The clinical symptomatology indicates that this case cannot be considered as a subtype of inherited ichthyosis group, but suggests a new syndrome as a separate nosologic entity. Two previously reported cases with possibly the same syndrome also had ichthyosis associated with variable endocrinopathy. Thorough endocrinological evaluation and appropriate intervention in patients of ichthyosis with short stature may reduce the morbidity associated with retarded skeletal growth and gonadal maturation.
一名15岁男性自婴儿期起就患有鱼鳞病,伴有全垂体功能减退、身材矮小、膝外翻、青春期延迟、阴囊高位回缩睾丸、智力发育迟缓及角膜混浊。他还反复发生头癣和体癣。临床症状表明,该病例不能被视为遗传性鱼鳞病组的一个亚型,而是提示一种新的综合征,作为一个独立的疾病实体。另外两个先前报道的可能患有相同综合征的病例也有鱼鳞病合并多种内分泌病。对身材矮小的鱼鳞病患者进行全面的内分泌评估和适当干预,可能会降低与骨骼生长迟缓和性腺成熟延迟相关的发病率。