Sánchez-Juan Pascual, Bishop Matthew T, Green Alison, Giannattasio Claudia, Arias-Vasquez Alejandro, Poleggi Anna, Knight Richard S G, van Duijn Cornelia M
Institute for Formation and Research of the Fundación Marqués de Valdecilla (IFIMAV), Santander, Spain.
BMC Med Genet. 2007 Dec 11;8:77. doi: 10.1186/1471-2350-8-77.
A polymorphism at codon 129 of the prion protein gene (PRNP) is the only well-known genetic risk factor for Creutzfeldt-Jakob disease (CJD). However, there is increasing evidence that other loci outside the PRNP open reading frame might play a role in CJD aetiology as well.
We studied tau protein gene (MAPT) haplotypic variations in a population of sporadic and variant CJD patients. We tested 6 MAPT haplotype tagging SNPs (htSNPs) in a Dutch population-based sample of sporadic CJD (sCJD) patients and a cognitively normal control group of similar age distribution. We genotyped the same polymorphisms in two other sample groups of sCJD cases from Italy and the UK. In addition, we compared MAPT haplotypes between sCJD and variant CJD (vCJD) patients.
Single locus and haplotype analyses did not detect any significant difference between sCJD cases and controls. When we compared MAPT haplotypes between sCJD and variant CJD (vCJD) patients, we found that two of them were represented differently (H1f: 8% in sCJD versus 2% in vCJD; H1j:1% in sCJD versus 7% in vCJD). However, these two haplotypes were rare in both groups of patients, and taking the small sample sizes into account, we cannot exclude that the differences are due to chance. None of the p-values remained statistically significant after applying a multiple testing correction.
Our study shows no evidence for an association between MAPT gene variations and sCJD, and some weak evidence for an association to vCJD.
朊蛋白基因(PRNP)第129密码子处的多态性是克雅氏病(CJD)唯一广为人知的遗传风险因素。然而,越来越多的证据表明,PRNP开放阅读框之外的其他基因座可能也在CJD病因中发挥作用。
我们研究了散发型和变异型CJD患者群体中tau蛋白基因(MAPT)单倍型变异情况。我们在荷兰基于人群的散发型CJD(sCJD)患者样本以及年龄分布相似的认知正常对照组中检测了6个MAPT单倍型标签单核苷酸多态性(htSNP)。我们在另外两个分别来自意大利和英国的sCJD病例样本组中对相同的多态性进行了基因分型。此外,我们比较了sCJD和变异型CJD(vCJD)患者之间的MAPT单倍型。
单基因座和单倍型分析未发现sCJD病例与对照组之间存在任何显著差异。当我们比较sCJD和变异型CJD(vCJD)患者之间的MAPT单倍型时,我们发现其中两种单倍型的比例存在差异(H1f:sCJD中为8%,vCJD中为2%;H1j:sCJD中为1%,vCJD中为7%)。然而,这两种单倍型在两组患者中都很罕见,考虑到样本量较小,我们不能排除这些差异是偶然造成的。在应用多重检验校正后,没有一个p值仍具有统计学意义。
我们的研究没有发现MAPT基因变异与sCJD之间存在关联的证据,仅有一些微弱证据表明其与vCJD存在关联。