Hanebutt F L, Rolf N, Loesel A, Kuhlisch E, Siegert G, Knoefler R
Department of Pediatric Hematology and Oncology, University Hospital Carl Gustav Carus of Technical University Dresden, Dresden, Germany.
Haemophilia. 2008 May;14(3):524-30. doi: 10.1111/j.1365-2516.2008.01672.x. Epub 2008 Feb 18.
Desmopressin (DDAVP) affects haemostasis by the release of von Willebrand factor and coagulation factor VIII from endothelium. The aim of the study was to evaluate the results of DDAVP testing in paediatric patients with congenital bleeding disorders. Forty-one patients consisting of children with von Willebrand's disease (VWD, n = 26) and platelet function defects (PFD, n = 15) received DDAVP intravenously at a dosage of 0.3 mug/kg over 30 min. FVIII activity (FVIII), von Willebrand factor antigen (VWF:Ag), collagen-binding activity (VWF:CB) and PFA 100((R)) closure times (CT) were measured before, 60, 120 and 240 min after DDAVP. In VWD, the VWF:Ag increased threefold until 60 min and then it decreased continuously. Compared with baseline, VWF:Ag was significantly higher at 60 and 120 min but not at 240 min. In contrast, in PFD, the peak of VWF:Ag was reached after 120 min. Two hundred and forty minutes after DDAVP, the mean was still significantly elevated compared with baseline values. The course of VWF:CB corresponded to that of VWF:Ag. In patients with VWD and PFD, FVIII rose two- to threefold within 2 h after DDAVP. CT in patients with VWD shortened markedly within 120 min and then rose again. In all children with PFD, except one non-responder, the CT shortened within 240 min after DDAVP. Two non-responders with VWD were identified by the failed increase of VWF:Ag, VWF:CB and by prolonged CT. Haemostatic effects of DDAVP differ interindividually and dependent on the coagulation disorder. DDAVP was effective in most, but not in all patients. DDAVP testing is recommended to determine the individual haemostatic response.
去氨加压素(DDAVP)通过促使血管性血友病因子和凝血因子VIII从内皮细胞释放来影响止血。本研究的目的是评估DDAVP检测在患有先天性出血性疾病的儿科患者中的结果。41例患者包括血管性血友病(VWD,n = 26)和血小板功能缺陷(PFD,n = 15)的儿童,以0.3μg/kg的剂量在30分钟内静脉注射DDAVP。在DDAVP给药前、给药后60、120和240分钟测量FVIII活性(FVIII)、血管性血友病因子抗原(VWF:Ag)、胶原结合活性(VWF:CB)和PFA 100(R)封闭时间(CT)。在VWD患者中,VWF:Ag在60分钟前增加了三倍,然后持续下降。与基线相比,VWF:Ag在60和120分钟时显著升高,但在240分钟时未升高。相比之下,在PFD患者中,VWF:Ag在120分钟后达到峰值。DDAVP给药240分钟后,平均值仍比基线值显著升高。VWF:CB的变化过程与VWF:Ag一致。在VWD和PFD患者中,DDAVP给药后2小时内FVIII升高了两到三倍。VWD患者的CT在120分钟内显著缩短,然后再次升高。在所有PFD儿童中,除一名无反应者外,CT在DDAVP给药后240分钟内缩短。两名VWD无反应者通过VWF:Ag、VWF:CB未增加以及CT延长得以识别。DDAVP的止血效果存在个体差异,且取决于凝血障碍。DDAVP对大多数但并非所有患者有效。建议进行DDAVP检测以确定个体的止血反应。