Ko T M, Hsieh F J, Hsu P M, Lee T Y
Department of Obstetrics and Gynecology, College of Medicine, National Taiwan University, Republic of China.
Am J Med Genet. 1991 Jun 1;39(3):317-20. doi: 10.1002/ajmg.1320390314.
alpha-Thalassemia hydrops fetalis is a common disorder in Taiwan. The condition causes perinatal death and many maternal obstetrical complications. In order to determine the molecular defects of this condition in Chinese, 87 unrelated families with this disorder were collected in the past 4 years. The molecular defects were studied by Southern blotting and DNA hybridization with phi zeta 1-globin gene and LO (a 0.4 kb BamHI/EcoRI fragment in the 5' flanking region of the zeta 2-globin gene) probes. Eighty-one (93.1%) fetuses had homozygous Southeast Asian deletion (- -SEA/- -SEA). Five (5.7%) fetuses were compound heterozygotes for the Southeast Asian deletion and Thailand deletion (- -SEA/- -THAI). The remaining fetus was a compound heterozygote for the Southeast Asian deletion and an uncharacterized nondeletional defect (- -SEA/(alpha alpha)Th). The molecular defects of alpha-thalassemia hydrops fetalis in Chinese are heterogeneous. This fact has important implications for genetic counseling and prenatal diagnosis.
α-地中海贫血胎儿水肿综合征在台湾是一种常见疾病。这种病症会导致围产期死亡以及许多产妇产科并发症。为了确定中国人中这种病症的分子缺陷,在过去4年里收集了87个患有该病症的无血缘关系家庭。通过Southern印迹法以及用φζ1-珠蛋白基因和LO(ζ2-珠蛋白基因5'侧翼区域中的一个0.4 kb BamHI/EcoRI片段)探针进行DNA杂交来研究分子缺陷。81例(93.1%)胎儿为纯合东南亚缺失型(--SEA/--SEA)。5例(5.7%)胎儿是东南亚缺失型和泰国缺失型的复合杂合子(--SEA/--THAI)。其余胎儿是东南亚缺失型和一种未明确的非缺失型缺陷的复合杂合子(--SEA/(αα)Th)。中国人中α-地中海贫血胎儿水肿综合征的分子缺陷是异质性的。这一事实对遗传咨询和产前诊断具有重要意义。