Vidovic Maria, Chen Ming-Ming, Lu Qun-Ying, Kalloniatis Katherine F, Martin Ben M, Tan Abel H Y, Lynch Celina, Croaker G David H, Cass Daniel T, Song Zan-Min
Division of Neuroscience, John Curtin School of Medical Research, Australian National University, Canberra, ACT 0200, Australia.
Cell Mol Neurobiol. 2008 Dec;28(8):1129-38. doi: 10.1007/s10571-008-9292-z. Epub 2008 Aug 6.
Endothelins regulate cellular functions in the mammalian brain through the endothelin receptors A and B (EDNRA and EDNRB). In this study, we investigated the role of EDNRB on cell proliferation in the cerebellum by using the spotting lethal (sl) rat, which carries a naturally occurring deletion in the EDNRB gene. Proliferating cells in the three genotypes, wild-type (+/+), heterozygous (+/sl) and homozygous mutant (sl/sl) rats were labelled by intraperitoneal injection of 5-bromo-2'-deoxyuridine (BrdU) at postnatal day 2. The density of BrdU-positive cells (per mm(2)) in the external germinal layer of sl/sl rats (Mean +/- SEM, 977 +/- 388) was significantly reduced compared to +/+ (4915 +/- 631) and +/sl (2304 +/- 557) rats. Subsequently, we examined the effects of EDNRB mutation on neural apoptosis by terminal deoxynucleotidyltransferase-mediated dUTP nick end-labelling assay. This showed that the density of apoptotic cells in the cerebella of sl/sl rats (9.3 +/- 0.5/mm(2)) was significantly more increased than +/+ rats (4 +/- 0.7). The expression of brain-derived neurotrophic factor (BDNF) and glial cell line-derived neurotrophic factor (GDNF) were measured with standard ELISA, but were unchanged in all genotypes. These results suggest that ENDRB mediates neural proliferation and have anti-apoptotic effects in the cerebellum of the postnatal rat, and that these effects are independent of changes in the expression of BDNF and GDNF. Our findings will lead to better understanding of the morphological changes in the cerebellum of Hirschsprung's disease patients with congenital EDNRB mutation.
内皮素通过内皮素受体A和B(EDNRA和EDNRB)调节哺乳动物大脑中的细胞功能。在本研究中,我们利用斑点致死(sl)大鼠研究了EDNRB在小脑细胞增殖中的作用,该大鼠的EDNRB基因存在自然缺失。在出生后第2天,通过腹腔注射5-溴-2'-脱氧尿苷(BrdU)对三种基因型(野生型(+/+)、杂合子(+/sl)和纯合突变体(sl/sl))大鼠的增殖细胞进行标记。与+/+(4915±631)和+/sl(2304±557)大鼠相比,sl/sl大鼠外颗粒层中BrdU阳性细胞的密度(每平方毫米)显著降低(平均±标准误,977±388)。随后,我们通过末端脱氧核苷酸转移酶介导的dUTP缺口末端标记法检测了EDNRB突变对神经细胞凋亡的影响。结果表明,sl/sl大鼠小脑凋亡细胞的密度(9.3±0.5/平方毫米)比+/+大鼠(4±0.7)显著增加。采用标准酶联免疫吸附测定法测量脑源性神经营养因子(BDNF)和胶质细胞系源性神经营养因子(GDNF)的表达,但在所有基因型中均未发生变化。这些结果表明,EDNRB介导神经增殖并对出生后大鼠的小脑具有抗凋亡作用,且这些作用与BDNF和GDNF表达的变化无关。我们的研究结果将有助于更好地理解先天性EDNRB突变的先天性巨结肠病患者小脑的形态学变化。