Kinomura Masaru, Maeshima Yohei, Kodera Ryo, Morinaga Hiroshi, Saito Daisuke, Nakao Kazushi, Yanai Hiroyuki, Sada Kenei, Sugiyama Hitoshi, Makino Hirofumi
Department of Medicine and Clinical Science, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences, 2-5-1 Shikata-cho, Okayama, 700-8558, Japan.
Department of Pathology, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences, Okayama, Japan.
Clin Exp Nephrol. 2009 Aug;13(4):378-384. doi: 10.1007/s10157-009-0166-6. Epub 2009 Apr 15.
We report a case of immunotactoid glomerulopathy (ITG) with cerebral hemorrhage and hypocomplementemia, with successful therapeutic outcome following the corticosteroids and antihypertensive treatment. A 70-year-old man presented with facial edema in October 2006. One day prior to his referral, he experienced speech disturbance, headache, and vomiting, and on the next day he was referred to our hospital. The laboratory examination revealed massive proteinuria (11.3 g/day) and hematuria. The total serum hemolytic complement (CH50) was decreased to 23 U/ml and C4 component was decreased to 7.5 mg/dl, whereas C3 component remained within normal limits (82 mg/dl). Brain computed tomography scan showed high-density lesions in the left parieto-occipital area suggesting subcortical cerebral hemorrhage. Renal biopsy revealed diffuse subendothelial PAS-positive depositions. Immunofluorescence studies revealed intensive deposition of IgG, IgA, C3, C1q, Fibrinogen, and kappa light chain with granular pattern in the capillary and mesangial area. Electron microscopic examination revealed regularly arranged microtubular deposits, appearing as 21-33 nm in diameter. Based on these findings, this patient was diagnosed as ITG complicated with cerebral hemorrhage and hypocomplementemia. He received oral prednisolone (30 mg/day), resulting in reduction of proteinuria, improvement of hypocomplementemia, and prevention of renal functional deterioration. This case demonstrates that accurate diagnosis of ITG may result in successful therapeutic outcome.
我们报告一例免疫触须样肾小球病(ITG)合并脑出血和低补体血症的病例,经皮质类固醇和抗高血压治疗后取得了成功的治疗效果。一名70岁男性于2006年10月出现面部水肿。在转诊前一天,他出现言语障碍、头痛和呕吐,次日被转诊至我院。实验室检查显示大量蛋白尿(11.3g/天)和血尿。血清总溶血补体(CH50)降至23U/ml,C4成分降至7.5mg/dl,而C3成分仍在正常范围内(82mg/dl)。脑部计算机断层扫描显示左顶枕区有高密度病变,提示皮质下脑出血。肾活检显示弥漫性内皮下PAS阳性沉积物。免疫荧光研究显示IgG、IgA、C3、C1q、纤维蛋白原和κ轻链在毛细血管和系膜区呈颗粒状密集沉积。电子显微镜检查显示有规则排列的微管沉积物,直径为21-33nm。基于这些发现,该患者被诊断为ITG合并脑出血和低补体血症。他接受了口服泼尼松龙(30mg/天)治疗,导致蛋白尿减少、低补体血症改善,并预防了肾功能恶化。该病例表明,ITG的准确诊断可能会带来成功的治疗结果。