Yi S, Takahashi K, Naito M, Tashiro F, Wakasugi S, Maeda S, Shimada K, Yamamura K, Araki S
Second Department of Pathology, Kumamoto University Medical School, Japan.
Am J Pathol. 1991 Feb;138(2):403-12.
To analyze the pathologic processes of amyloid deposition in type I familial amyloidotic polyneuropathy (FAP), mice were made transgenic by introducing the human mutant transthyretin (TTR) gene. In these transgenic mice, amyloid deposition started in the gastrointestinal tract, cardiovascular system, and kidneys 6 months after birth and extended to various other organs and tissues with advancing age. At age 24 months, the pattern of amyloid deposition was similar to that observed in human autopsy cases of FAP, except for its absence in the choroid plexus and in the peripheral and autonomic nervous systems. Amyloid deposition was shown to be composed of human mutant TTR and, in addition, mouse serum amyloid P component. These results clearly indicate that human variant TTR produced in transgenic mice deposits is a major component of amyloid fibrils in various organs and tissues. Thus this animal model is useful for analyzing how amyloid deposition initiates and proceeds in FAP.
为分析I型家族性淀粉样多神经病(FAP)中淀粉样沉积的病理过程,通过导入人突变型转甲状腺素蛋白(TTR)基因使小鼠转基因。在这些转基因小鼠中,淀粉样沉积在出生后6个月开始于胃肠道、心血管系统和肾脏,并随着年龄增长扩展到其他各种器官和组织。在24个月龄时,淀粉样沉积模式与FAP人类尸检病例中观察到的相似,除了脉络丛以及外周和自主神经系统中不存在。淀粉样沉积显示由人突变型TTR组成,此外还有小鼠血清淀粉样P成分。这些结果清楚地表明,转基因小鼠中产生的人变异TTR沉积物是各种器官和组织中淀粉样纤维的主要成分。因此,这种动物模型对于分析FAP中淀粉样沉积如何启动和进展是有用的。