Department of Internal Medicine, University Hospital, Boulevard Fleming, Besançon 25030, France.
J Clin Neurosci. 2010 Mar;17(3):389-91. doi: 10.1016/j.jocn.2009.06.015. Epub 2010 Jan 13.
Stiff-person syndrome (SPS) is an autoimmune neurological disorder characterized by stiffness of the skeletal muscle with superimposed spasms and production of autoantibodies to glutamic acid decarboxylase (GAD) and amphiphysin. The disorder results from B cell-mediated clonal production of autoantibodies, requiring treatment with immunosuppressors; however, treatment results have been somewhat inconsistent. We report the results of rituximab treatment in a patient with SPS associated with a thymoma, diabetes mellitus, autoimmune thyroiditis and the presence of anti-GAD and anti-amphiphysin autoantibodies. The patient experienced a partial improvement following a thymectomy and the administration of prednisone, intravenous immunoglobulins and mycophenolate mofetil. Treatment with rituximab was followed by a complete sustained remission and the disappearance of serum anti-amphiphysin antibodies.
僵人综合征(SPS)是一种自身免疫性神经系统疾病,其特征为骨骼肌僵硬,伴有痉挛,并产生谷氨酸脱羧酶(GAD)和 amphiphysin 的自身抗体。该疾病是由 B 细胞介导的克隆性产生自身抗体引起的,需要免疫抑制剂治疗;然而,治疗效果有些不一致。我们报告了一例伴有胸腺瘤、糖尿病、自身免疫性甲状腺炎以及存在抗 GAD 和抗 amphiphysin 自身抗体的 SPS 患者接受利妥昔单抗治疗的结果。该患者在接受胸腺切除术、泼尼松、静脉注射免疫球蛋白和霉酚酸酯治疗后,症状部分改善。利妥昔单抗治疗后,患者完全持续缓解,血清抗 amphiphysin 抗体消失。