Department of Paediatrics, Emma Children's Hospital, Amsterdam, The Netherlands.
Placenta. 2010 Apr;31(4):344-6. doi: 10.1016/j.placenta.2010.02.004. Epub 2010 Mar 1.
There are only a few reports on the histology of placental tissue of pregnancies from mothers with Fabry disease. Fabry disease is a lysosomal disorder caused by alpha-galactosidase A deficiency. Extensive glycosphingolipid (GSL) accumulation in fetal and maternal placenta tissue obtained from a Fabry mother and her affected male newborn has previously been reported. Here we report the evaluation of placenta tissue of two pregnancies in Fabry mothers, one of an unaffected male newborn (placenta A) and one of an affected female newborn (placenta B). The mother of the female affected offspring was treated with recombinant alpha-galactosidase A (enzyme replacement therapy, ERT) during the pregnancy (placenta B). Storage material was only detected in smooth muscle cells of the umbilical cord of placenta B. No accumulation was seen in both placentae. Combing these results with the outcome in two earlier described placentae, a heterogeneous picture emerges. This may be due to differences in disease severity in the mothers or severity of disease in their offspring. In addition, a possible effect of ERT on placental GSL accumulation could also explain lack of GSL storage in placenta B.
关于法布瑞病(Fabry disease)母亲妊娠的胎盘组织的组织学,仅有少数报道。法布瑞病是一种溶酶体贮积病,由α-半乳糖苷酶 A 缺乏引起。此前曾有报道称,在法布瑞病母亲及其患病男婴的胎儿和母亲胎盘组织中,广泛存在糖鞘脂(glycosphingolipid,GSL)堆积。在此,我们报告了对两名法布瑞病母亲妊娠胎盘组织的评估,其中一名新生儿为正常男性(胎盘 A),另一名为患病女性(胎盘 B)。患病女婴的母亲在妊娠期间接受了重组α-半乳糖苷酶 A(酶替代疗法,ERT)治疗(胎盘 B)。仅在胎盘 B 的脐带平滑肌细胞中检测到贮存物质。在两个胎盘组织中均未发现堆积。将这些结果与之前描述的两个胎盘的结果相结合,呈现出一种不均匀的情况。这可能是由于母亲疾病严重程度的差异或其子女疾病严重程度的差异所致。此外,ERT 对胎盘 GSL 堆积的可能影响也可以解释胎盘 B 中缺乏 GSL 贮存的原因。