一名患有左肺动脉血栓形成和左肺发育不全的新生儿：病例报告。
A neonate with left pulmonary artery thrombosis and left lung hypoplasia: a case report.
作者信息
Elhassan Nahed O, Sproles Christi, Sachdeva Ritu, Bhutta Sadaf T, Szabo Joanne S
机构信息
Department of Pediatrics, Neonatology, University of Arkansas for Medical Sciences, College of Medicine, Arkansas Children's Hospital, 1 Children's Way, Slot 512-5, Little Rock, AR 72202-3591, USA.
出版信息
J Med Case Rep. 2010 Aug 23;4:284. doi: 10.1186/1752-1947-4-284.
INTRODUCTION
Spontaneous intrauterine arterial thrombosis and congenital pulmonary hypoplasia are rare conditions and have not been reported to occur together. The literature rather includes two reports of babies with neonatal pulmonary artery occlusion and post-infarction cysts of the lungs.
CASE PRESENTATION
We report a case of a live Caucasian male newborn with left lung hypoplasia that occurred in association with left pulmonary artery thrombosis. Despite a critical neonatal course, including extracorporeal membrane oxygenation, this infant is alive and well at 18 months of age without any neurodevelopmental sequelae or reactive airway disease.
CONCLUSION
This association suggests the possibility of an intrauterine vascular event between the fifth and eighth weeks of gestation during early pulmonary artery and lung development.
引言
自发性子宫内动脉血栓形成和先天性肺发育不全是罕见病症，尚未有两者同时发生的报道。文献中倒是有两篇关于患有新生儿肺动脉闭塞和肺梗死后期囊肿婴儿的报道。
病例介绍
我们报告一例存活的白种男婴，其左肺发育不全与左肺动脉血栓形成有关。尽管经历了包括体外膜肺氧合在内的危急新生儿病程，但该婴儿在18个月大时仍健康存活，无任何神经发育后遗症或反应性气道疾病。
结论
这种关联提示在妊娠第5至8周早期肺动脉和肺发育期间发生子宫内血管事件的可能性。
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