Department of Radiology and Diagnostic Imaging, University of Alberta, Edmonton, Alberta, Canada.
Pediatr Radiol. 2011 Nov;41(11):1476-80. doi: 10.1007/s00247-011-2030-6. Epub 2011 Mar 11.
We report an unusual case of chronic mesenteric ischemia presenting in a 12-year-old girl with idiopathic infantile arterial calcinosis (IIAC). This is the first reported case in the literature of chronic mesenteric ischemia in the setting of IIAC. The girl presented with a classical history of postprandial abdominal pain. Imaging demonstrated significant stenoses of the celiac axis, superior mesenteric artery (SMA) and inferior mesenteric artery (IMA). Angioplasty of the celiac axis and SMA was attempted, with successful dilation of the SMA only. At 3-, 6- and 12-month follow-ups, the child's symptoms had almost resolved. This case report has three important ramifications: chronic mesenteric ischemia is a possible clinical presentation in children with IACC, pre-angioplasty imaging is important in guiding treatment approach, and angioplasty was effective in this case of chronic mesenteric ischemia and offers hope for other similarly affected children.
我们报告了一例罕见的慢性肠系膜缺血病例,该病例发生在一名 12 岁的特发性婴儿性动脉钙化(IIAC)女孩中。这是文献中首例报告的 IIAC 合并慢性肠系膜缺血病例。该女孩表现出典型的餐后腹痛病史。影像学检查显示腹腔动脉、肠系膜上动脉(SMA)和肠系膜下动脉(IMA)存在明显狭窄。尝试对腹腔动脉和 SMA 进行血管成形术,但仅成功扩张了 SMA。在 3、6 和 12 个月的随访中,患儿的症状几乎完全缓解。本病例报告有三个重要的意义:慢性肠系膜缺血是儿童 IIAC 的一种可能的临床表现,血管成形术前的影像学检查对指导治疗方法很重要,而且血管成形术在这种慢性肠系膜缺血病例中是有效的,为其他同样受影响的儿童带来了希望。