Meyer-Marcotty M V, Kollewe K, Dengler R, Grigull L, Altintas M A, Vogt P M
Klinik für Plastische-, Hand- und Wiederherstellungschirurgie, Medizinische Hochschule Hannover.
Handchir Mikrochir Plast Chir. 2012 Jan;44(1):23-8. doi: 10.1055/s-0032-1301918. Epub 2012 Mar 1.
Carpal tunnel syndrome is common in children with mucopolysaccharidosis type 1H (MPS type 1H). Clinical signs of carpal tunnel syndrome are frequently absent in these children and it is often very difficult to perform and interpret neurophysiological investigations. In this article we wish to present our experience and results regarding the diagnosis and postoperative results after decompression of the median nerve.In an interdisciplinary set-up we are currently treating 11 MPS type 1H children following blood stem cell transplantation. 7 patients were operated 12 times (5 bilateral operations) because of a carpal tunnel syndrome (age at the time of operation 83,3 months, (43-143 months), 2 male, 5 female). 6 patients had a follow up after 23,7 months (9-59 months). 6 patients had a histological analysis of the flexor retinaculum. Three patients had a postoperative neurophysiological investigation.Each of the operated patients had at least 1 preoperative clinical sign of a carpal tunnel syndrome. We found at least 1 pathological finding in motor and sensory nerve conduction studies in each patient. 6 of the 7 children operated on were symptom-free at postoperative follow-up. 1 of the 3 patients with a postoperative neurophysiological follow up showed a deterioration of the nerve conduction studies. This patient was free of symptoms postoperatively. Biopsy of the flexor retinaculum confirmed abundant proteoglycan deposition. We had neither postoperative complications nor were revisional operations necessary.The Diagnosis of a carpal tunnel syndrome in children with MPS Typ 1H needs a thorough medical history, the correct interpretation of the clinical symptoms and sophisticated nerve conduction studies. Wether the improvement of the postoperative clinical situation lasts has to be evaluated in a long term investigation especially because in one patient in our group we saw a deterioration of the nerve conduction studies postoperatively.
1H型黏多糖贮积症(MPS 1H)患儿常患腕管综合征。这些患儿往往没有腕管综合征的临床体征,而且进行神经生理学检查并对结果进行解读常常非常困难。在本文中,我们希望介绍我们在正中神经减压术后的诊断及术后结果方面的经验和成果。
在一个跨学科的医疗团队中,我们目前正在对11名接受造血干细胞移植后的MPS 1H患儿进行治疗。7名患者因腕管综合征接受了12次手术(5次双侧手术)(手术时年龄为83.3个月,范围43 - 143个月,2名男性,5名女性)。6名患者在术后23.7个月(9 - 59个月)进行了随访。6名患者对屈肌支持带进行了组织学分析。3名患者进行了术后神经生理学检查。
每例接受手术的患者术前至少有1项腕管综合征的临床体征。我们发现每名患者在运动和感觉神经传导研究中至少有1项病理表现。7名接受手术的患儿中有6名在术后随访时无症状。3名接受术后神经生理学随访患者中的1名显示神经传导研究结果恶化。该患者术后无症状。屈肌支持带活检证实有大量蛋白聚糖沉积。我们既没有术后并发症,也无需再次手术。
诊断MPS 1H型患儿的腕管综合征需要详细的病史、对临床症状的正确解读以及精密的神经传导研究。术后临床状况的改善是否持续需要进行长期研究评估,特别是因为在我们的一组患者中,有1例患者术后神经传导研究结果出现恶化。