Mavrikakis M E, Sfikakis P P, Kontoyannis D A, Antoniades L G, Tsakanikas C
Department of Clinical Therapeutics, Alexandra Hospital, Athens Medical School, Greece.
Ann Rheum Dis. 1990 Nov;49(11):942-3. doi: 10.1136/ard.49.11.942.
A 21 year old man with a family history of gout and neurological deficits, developed severe idiopathic congestive cardiomyopathy after a long history of typical gouty attacks and neurological abnormalities. Clinical and laboratory evaluations showed borderline mental retardation, ataxia, sensorineural deafness, marked hyperuricaemia, and excessive uric acid excretion in the presence of impaired renal function. None of the known causes of cardiomyopathy was found. Even though red cell hypoxanthine guanine phosphoribosyltransferase enzyme activity was normal, this case probably represents an inborn error of purine metabolism. The association of cardiomyopathy with gout is very unusual. Previously it has been only once described in a single case.
一名21岁男性,有痛风和神经功能缺损家族史,在经历长期典型痛风发作和神经异常病史后,发展为严重特发性充血性心肌病。临床和实验室评估显示边缘智力迟钝、共济失调、感音神经性耳聋、明显高尿酸血症,以及在肾功能受损情况下尿酸排泄过多。未发现心肌病的已知病因。尽管红细胞次黄嘌呤鸟嘌呤磷酸核糖转移酶活性正常,但该病例可能代表嘌呤代谢先天性缺陷。心肌病与痛风的关联非常罕见。此前仅在一例中被描述过一次。