Department of Physiology, University of Alberta, Edmonton, Alberta, Canada.
Am J Physiol Cell Physiol. 2012 Sep 1;303(5):C554-66. doi: 10.1152/ajpcell.00124.2012. Epub 2012 Jun 27.
Distal renal tubular acidosis (dRTA) can be caused by mutations in the gene encoding the anion exchanger 1 (AE1) and is characterized by defective urinary acidification, metabolic acidosis, and renal stones. AE1 is expressed at the basolateral membrane of type A intercalated cells in the renal cortical collecting duct (kAE1). Two dRTA mutations result in the carboxyl-terminal truncation of kAE1; in one case, the protein trafficked in a nonpolarized way in epithelial cells. A recent yeast two-hybrid assay showed that the carboxyl-terminal cytosolic domain of AE1 interacts with adaptor protein complex 1 (AP-1A) subunit μ1A (mu-1A; Sawasdee N, Junking M, Ngaojanlar P, Sukomon N, Ungsupravate D, Limjindaporn T, Akkarapatumwong V, Noisakran S, Yenchitsomanus PT. Biochem Biophys Res Commun 401: 85-91, 2010). Here, we show the interaction between kAE1 and mu-1A and B in vitro by reciprocal coimmunoprecipitation in epithelial cells and in vivo by coimmunoprecipitation from mouse kidney extract. When endogenous mu-1A (and to a lesser extent mu-1B) was reduced, kAE1 protein was unable to traffic to the plasma membrane and was rapidly degraded via a lysosomal pathway. Expression of either small interfering RNA-resistant mu-1A or mu-1B stabilized kAE1 in these cells. We also show that newly synthesized kAE1 does not traffic through recycling endosomes to the plasma membrane, suggesting that AP-1B, located in recycling endosomes, is not primarily involved in trafficking of newly synthesized kAE1 when AP-1A is present in the cells. Our data demonstrate that AP-1A regulates processing of the basolateral, polytopic membrane protein kAE1 to the cell surface and that both AP-1A and B adaptor complexes are required for normal kAE1 trafficking.
远端肾小管性酸中毒(dRTA)可由编码阴离子交换器 1(AE1)的基因突变引起,其特征为尿酸化缺陷、代谢性酸中毒和肾结石。AE1 在肾皮质集合管的 A 型闰细胞基底外侧膜表达(kAE1)。两种 dRTA 突变导致 kAE1 的羧基末端截断;在一种情况下,该蛋白在上皮细胞中以非极化方式运输。最近的酵母双杂交测定显示,AE1 的羧基末端胞质域与衔接蛋白复合物 1(AP-1A)亚基 μ1A(mu-1A;Sawasdee N、Junking M、Ngaojanlar P、Sukomon N、Ungsupravate D、Limjindaporn T、Akkarapatumwong V、Noisakran S、Yenchitsomanus PT。生物化学与生物物理研究通讯 401:85-91,2010)相互作用。在这里,我们通过上皮细胞中的相互共免疫沉淀实验和体内通过从鼠肾提取物中的共免疫沉淀实验显示了 kAE1 与 mu-1A 和 B 之间的体外相互作用。当内源性 mu-1A(和较少程度的 mu-1B)减少时,kAE1 蛋白无法转运到质膜,并通过溶酶体途径迅速降解。这些细胞中小干扰 RNA 抗性的 mu-1A 或 mu-1B 的表达稳定了 kAE1。我们还表明,新合成的 kAE1 不会通过再循环内体运输到质膜,这表明位于再循环内体中的 AP-1B 当 AP-1A 存在于细胞中时,并不是新合成的 kAE1 运输的主要参与者。我们的数据表明,AP-1A 调节基底外侧、多拓扑膜蛋白 kAE1 到质膜的加工,并且正常的 kAE1 运输需要 AP-1A 和 B 衔接复合物。