Carrascosa Miguel F, Larroque Isabel Celemín, Rivero Juan-Luis García, García José-Antonio Saiz-Quevedo, Hoz Marta Cano, Ares Miguel Ares, López Xabier Arrastio, Caviedes José-Ramón Salcines
Department of Internal Medicine, Hospital of Laredo, Laredo, Spain.
BMJ Case Rep. 2010 Nov 29;2010:bcr0520102961. doi: 10.1136/bcr.05.2010.2961.
The authors report a case of severe pulmonary arterial hypertension (PAH) in a 75-year-old woman who had received a diagnosis of neurofibromatosis type 1 (NF1) 23 years before. She presented with progressive dyspnoea and recurrent syncope. Even though the patient initially improved after starting supportive and specific treatment for PAH, she then deteriorated and died from respiratory failure 11 months after the diagnosis of PAH. Prompt recognition of such an unusual association between PAH and NF1 and appropriate therapeutic intervention could ameliorate quality of life and prolong survival in this patient population.
作者报告了一例75岁女性的严重肺动脉高压(PAH)病例,该患者23年前被诊断为1型神经纤维瘤病(NF1)。她出现进行性呼吸困难和反复晕厥。尽管患者在开始针对PAH的支持性和特异性治疗后最初有所改善,但随后病情恶化,在诊断为PAH后11个月死于呼吸衰竭。及时认识到PAH与NF1之间的这种不寻常关联并进行适当的治疗干预,可以改善该患者群体的生活质量并延长生存期。