Haroon Saroona, Hasan Sheema H
Department of Pathology and Microbiology, Aga Khan University Hospital, Stadium Road, P,O, Box 3500, Karachi, 74800, Pakistan.
J Med Case Rep. 2012 Aug 9;6:233. doi: 10.1186/1752-1947-6-233.
Lymphangioma circumscriptum is a rare benign skin disorder involving hamartomatous lymphatic malformation of deep dermal and subcutaneous lymphatic channels. It is a therapeutic challenge for the dermatologist when it occurs at common sites such as axilla, shoulder, groin and buttocks and a diagnostic challenge for the surgeon when it occurs at rare sites such as the scrotum. Surgical treatment is the most commonly used method to treat scrotal lymphangioma circumscriptum but there are high rates of recurrence.
We report the case of a 30-year-old Pakistani man who presented with scrotal swelling which was clinically misinterpreted as an infectious disorder. Later on re-resection of deeper tissue was performed to prevent recurrence. He is still being followed-up on a regular basis.
Awareness of the occurrence of lymphangioma circumscriptum in the scrotum in adult men without prior disease is mandatory to avoid missing the diagnosis and to ensure proper treatment.
局限性淋巴管瘤是一种罕见的良性皮肤疾病，涉及真皮深层和皮下淋巴管的错构瘤性淋巴畸形。当它发生在腋窝、肩部、腹股沟和臀部等常见部位时，对皮肤科医生来说是一个治疗挑战；而当它发生在阴囊等罕见部位时，对外科医生来说是一个诊断挑战。手术治疗是治疗阴囊局限性淋巴管瘤最常用的方法，但复发率很高。
我们报告一例30岁的巴基斯坦男性病例，该患者出现阴囊肿胀，临床上被误诊为感染性疾病。后来进行了更深层组织的再次切除以预防复发。他仍在定期接受随访。
对于成年男性无既往病史而出现阴囊局限性淋巴管瘤的情况，必须提高认识，以免漏诊并确保得到恰当治疗。
