Ludwig Kathrin, Salmaso Roberto, Cosmi Erich, Iaria Loredana, De Luca Alessandro, Margiotti Katia, Valentina Citton, Manara Renzo, Rugge Massimo
Department of Medicine (DIMED), Surgical Pathology and Cytopathology Unit, University of Padova, Padova, Italy.
Pediatr Dev Pathol. 2012 Nov-Dec;15(6):495-8. doi: 10.2350/12-03-1169-CR.1. Epub 2012 Aug 17.
Cantrell's pentalogy (CP) is a rare, mainly sporadic spectrum of congenital midline thoracoabdominal defects that includes sternal anomalies, ventral diaphragmatic hernia, partial absence of the pericardium, supraumbilical abdominal wall defects, and congenital heart malformations. The approximate incidence is 1 in 100 000, with a 2∶1 male predominance. A 25-year-old pregnant woman was referred to the Prenatal Diagnosis Unit of the University Hospital of Padua for multiple congenital malformations at 21 weeks of gestation. A level 2 ultrasound scan was performed and confirmed the presence of multiple anomalies compatible with the diagnosis of CP associated with complete ectopia cordis. Fetal autopsy furthermore revealed asplenia, which usually presents as part of the heterotaxia spectrum. To our knowledge, an association of CP and complete ectopia cordis with asplenia has never been reported so far.
坎特雷尔五联症(CP)是一种罕见的、主要为散发性的先天性胸腹部中线缺陷谱,包括胸骨异常、腹侧膈疝、部分心包缺如、脐上腹壁缺损和先天性心脏畸形。其发病率约为十万分之一,男性占比为2∶1。一名25岁孕妇在妊娠21周时因多发先天性畸形被转诊至帕多瓦大学医院产前诊断科。进行了二级超声扫描,证实存在与CP诊断相符的多种异常,并伴有完全性心脏异位。胎儿尸检进一步发现无脾,这通常是内脏异位谱的一部分。据我们所知,CP与完全性心脏异位合并无脾的关联迄今尚未见报道。