Suppr超能文献

一名慢性淋巴细胞白血病(CLL)患者,其核型为看似平衡的t(8;14)(q24.1;q32)且MYC表达阴性,存在涉及3'-IGH@的非典型重排以及在完整MYC上游至少400 Kb处的一个断点。

Atypical rearrangement involving 3'-IGH@ and a breakpoint at least 400 Kb upstream of an intact MYC in a CLL patient with an apparently balanced t(8;14)(q24.1;q32) and negative MYC expression.

作者信息

Amarillo Ina, Bui Peter H, Kantarci Sibel, Rao Nagesh, Shackley Brit S, García Rolando, Tirado Carlos A

机构信息

Clinical Molecular Cytogenetics Laboratory, Medicine, David Geffen UCLA School of Medicine, Los Angeles, CA, USA.

Department of Pathology & Laboratory, Medicine, David Geffen UCLA School of Medicine, Los Angeles, CA, USA.

出版信息

Mol Cytogenet. 2013 Feb 1;6(1):5. doi: 10.1186/1755-8166-6-5.

Abstract

The t(8;14)(q24.1;q32), the cytogenetic hallmark of Burkitt's lymphoma, is also found, but rarely, in cases of chronic lymphocytic leukemia (CLL). Such translocation typically results in a MYC-IGH@ fusion subsequently deregulating and overexpressing MYC on der 14q32. In CLL, atypical rearrangements resulting in its gain or loss, within or outside of IGH@ or MYC locus, have been reported, but their clinical significance remains uncertain. Herein, we report a 67 year-old male with complex cytogenetic findings of apparently balanced t(8;14) and unreported complex rearrangements of IGH@ and MYC loci. His clinical, morphological and immunophenotypic features were consistent with the diagnosis of CLL.Interphase FISH studies revealed deletions of 11q22.3 and 13q14.3, and an extra copy of IGH@, indicative of rearrangement. Karyotype analysis showed an apparently balanced t(8;14)(q24.1;q32). Sequential GPG-metaphase FISH studies revealed abnormal signal patterns: rearrangement of IGH break apart probe with the 5'-IGH@ on derivative 8q24.1 and the 3'-IGH@ retained on der 14q; absence of MYC break apart-specific signal on der 8q; and, the presence of unsplit 5'-MYC-3' break apart probe signals on der 14q. The breakpoint on 8q24.1 was found to be at least 400 Kb upstream of 5' of MYC. In addition, FISH studies revealed two abnormal clones; one with 13q14.3 deletion, and the other, with concurrent 11q deletion and atypical rearrangements. Chromosome microarray analysis (CMA) detected a 7.1 Mb deletion on 11q22.3-q23.3 including ATM, a finding consistent with FISH results. While no significant copy number gain or loss observed on chromosomes 8, 12 and 13, a 455 Kb microdeletion of uncertain clinical significance was detected on 14q32.33. Immunohistochemistry showed co-expression of CD19, CD5, and CD23, positive ZAP-70 expression and absence of MYC expression. Overall findings reveal an apparently balanced t(8;14) and atypical complex rearrangements involving 3'-IGH@ and a breakpoint at least 400 Kb upstream of MYC, resulting in the relocation of the intact 5'-MYC-3' from der 8q, and apposition to 3'-IGH@ at der 14q. This case report provides unique and additional cytogenetic data that may be of clinical significance in such a rare finding in CLL. It also highlights the utility of conventional and sequential metaphase FISH in understanding complex chromosome anomalies and their association with other clinical findings in patients with CLL. To the best of our knowledge, this is the first CLL reported case with such an atypical rearrangement in a patient with a negative MYC expression.

摘要

t(8;14)(q24.1;q32)是伯基特淋巴瘤的细胞遗传学特征,在慢性淋巴细胞白血病(CLL)病例中也有发现,但极为罕见。这种易位通常会导致MYC-IGH@融合,随后使14q32上的MYC失调并过度表达。在CLL中,已报道了导致IGH@或MYC基因座内部或外部出现其增加或缺失的非典型重排,但其临床意义仍不确定。在此,我们报告一名67岁男性,其具有明显平衡的t(8;14)以及未报道的IGH@和MYC基因座复杂重排的复杂细胞遗传学结果。他的临床、形态学和免疫表型特征与CLL诊断相符。间期荧光原位杂交(FISH)研究显示11q22.3和13q14.3缺失,以及IGH@额外拷贝,提示重排。核型分析显示明显平衡的t(8;14)(q24.1;q32)。连续的GPG中期FISH研究显示异常信号模式:IGH断裂分离探针重排,5'-IGH@位于衍生染色体8q24.1上,3'-IGH@保留在衍生染色体14q上;衍生染色体8q上无MYC断裂分离特异性信号;并且,衍生染色体14q上存在未分离的5'-MYC-3'断裂分离探针信号。发现8q24.1上的断点位于MYC 5'端上游至少400 Kb处。此外,FISH研究显示两个异常克隆;一个有13q14.3缺失,另一个同时有11q缺失和非典型重排。染色体微阵列分析(CMA)检测到11q22.3-q23.3上有一个7.1 Mb的缺失,包括ATM,这一发现与FISH结果一致。虽然在染色体8、12和13上未观察到显著的拷贝数增加或减少,但在14q32.33上检测到一个临床意义不确定的455 Kb微缺失。免疫组织化学显示CD19、CD5和CD23共表达,ZAP-70表达阳性且MYC表达缺失。总体结果显示明显平衡的t(8;14)以及涉及3'-IGH@和位于MYC上游至少400 Kb处的断点的非典型复杂重排,并导致完整的5'-MYC-3'从衍生染色体8q易位,并与衍生染色体14q上的3'-IGH@并列。本病例报告提供了独特且额外的细胞遗传学数据,这在CLL如此罕见的发现中可能具有临床意义。它还强调了传统和连续中期FISH在理解复杂染色体异常及其与CLL患者其他临床发现的关联方面的实用性。据我们所知,这是首例报道的CLL患者中具有这种非典型重排且MYC表达阴性的病例。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/4f07/3599416/021e136ec8dc/1755-8166-6-5-1.jpg

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验