Division of Cardiology, Department of Medicine, University of Colorado Denver, Anschutz Medical Campus, P-15 8006, B-139, Aurora, CO 80045, USA.
Biomed Res Int. 2013;2013:390493. doi: 10.1155/2013/390493. Epub 2012 Dec 5.
Malignant hyperthermia (MH) is a pharmacogenetic disorder most often linked to mutations in the type 1 ryanodine receptor (RyR1) or the skeletal L-type Ca(2+) channel (Ca(V)1.1). The only effective treatment for an MH crisis is administration of the hydantoin derivative Dantrolene. In addition to reducing voltage induced Ca(2+) release from the sarcoplasmic reticulum, Dantrolene was recently found to inhibit L-type currents in developing myotubes by shifting the voltage-dependence of Ca(V)1.1 channel activation to more depolarizing potentials. Thus, the purpose of this study was to obtain information regarding the mechanism of Dantrolene-induced inhibition of Ca(V)1.1. A mechanism involving a general depression of plasma membrane excitability was excluded because the biophysical properties of skeletal muscle Na(+) current in normal mouse myotubes were largely unaffected by exposure to Dantrolene. However, a role for RyR1 was evident as Dantrolene failed to alter the amplitude, voltage dependence and inactivation kinetics of L-type currents recorded from dyspedic (RyR1 null) myotubes. Taken together, these results suggest that the mechanism of Dantrolene-induced inhibition of the skeletal muscle L-type Ca(2+) current is related to altered communication between Ca(V)1.1 and RyR1.
恶性高热(MH)是一种遗传药理学疾病,通常与 1 型兰尼碱受体(RyR1)或骨骼肌 L 型 Ca2+通道(CaV1.1)的突变有关。MH 危机的唯一有效治疗方法是使用苯二氮䓬衍生物丹曲林。除了减少电压诱导的肌浆网 Ca2+释放外,丹曲林最近还被发现通过将 CaV1.1 通道激活的电压依赖性转移到更去极化的电位来抑制发育中的肌管中的 L 型电流。因此,本研究的目的是获得有关丹曲林抑制 CaV1.1 机制的信息。由于暴露于丹曲林中正常小鼠肌管中的骨骼肌 Na+电流的生物物理特性基本不受影响,因此排除了涉及质膜兴奋性普遍降低的机制。然而,RyR1 的作用是明显的,因为丹曲林未能改变从运动障碍(RyR1 缺失)肌管中记录的 L 型电流的幅度、电压依赖性和失活动力学。综上所述,这些结果表明,丹曲林抑制骨骼肌 L 型 Ca2+电流的机制与 CaV1.1 和 RyR1 之间通信的改变有关。