Nuffield Department of Clinical Neurosciences, John Radcliffe Hospital, University of Oxford, Oxford, United Kingdom.
Mov Disord. 2014 Jan;29(1):90-6. doi: 10.1002/mds.25626. Epub 2013 Sep 6.
Herpes simplex virus encephalitis (HSVE) is a devastating condition that relapses, often with a chorea in children, despite adequate antiviral treatment. At relapse, evidence of viral replication is frequently absent, suggesting that the relapse may be immune-mediated. Seven children who had a neurological relapse following their initial encephalitis, identified from 20 cases of pediatric HSVE, were studied. Serum and/or cerebrospinal fluid (CSF) were tested for N-methyl-D-aspartate receptor (NMDAR) and other antibodies previously reported in central nervous system autoimmunity. Five of the 7 relapsing children had choreoathetosis; 2 of these were NMDAR antibody-positive, 2 were negative (1 with HSV-positive CSF), and 1 was not available for testing. An additional patient, who relapsed with cognitive regression but with no movement disorder, was also NMDAR antibody-positive. In 2 of the NMDAR antibody-positive patients who were treated at relapse and in 1 who was treated only after 10 years of having a relapsing encephalopathy, a beneficial response was observed. Neurological relapses after HSVE may frequently be immune-mediated, particularly in children with chorea. NMDAR antibodies are common, and immunotherapy may be beneficial.
单纯疱疹病毒脑炎(HSVE)是一种破坏性疾病,尽管进行了充分的抗病毒治疗,但仍会复发,儿童常伴有舞蹈病。在复发时,通常缺乏病毒复制的证据,这表明复发可能是免疫介导的。从 20 例儿童 HSVE 中确定了 7 例在初次脑炎后出现神经学复发的儿童,对其进行了研究。对血清和/或脑脊液(CSF)进行了先前报道的中枢神经系统自身免疫中 N-甲基-D-天冬氨酸受体(NMDAR)和其他抗体的检测。7 例复发性儿童中有 5 例出现舞蹈手足徐动症;其中 2 例 NMDAR 抗体阳性,2 例为阴性(1 例 CSF 单纯疱疹病毒阳性),1 例未进行检测。另一位患者出现认知倒退但无运动障碍的复发,也呈 NMDAR 抗体阳性。在 2 例复发时接受治疗的 NMDAR 抗体阳性患者和 1 例在出现复发性脑病 10 年后接受治疗的患者中,观察到了有益的反应。HSVE 后的神经复发可能经常是免疫介导的,特别是在伴有舞蹈病的儿童中。NMDAR 抗体很常见,免疫治疗可能有益。