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一例酷似克罗恩病的小儿胃肠道担子菌病。儿科文献综述。

A case of pediatric gastrointestinal basidiobolomycosis mimicking Crohn`s disease. A review of pediatric literature.

作者信息

Al Asmi Mona M, Faqeehi Hassan Y, Alshahrani Dayel A, Al-Hussaini Abdulrahman A

机构信息

Department of Pediatrics, Children's Hospital, King Fahad Medical City, Riyadh, Kingdom of Saudi Arabia.

出版信息

Saudi Med J. 2013 Oct;34(10):1068-72.

Abstract

Basidiobolomycosis is a rare fungal infection caused by basidiobolus ranarum. The vast majority of gastrointestinal basidiobolomycosis cases were reported from tropical and subtropical regions. We report a Saudi pediatric patient with ileal basidiobolomycosis and initial clinical presentation mimicking acute appendicitis before being misdiagnosed as Crohn's disease. Our case is the first to report effective treatment of pediatric gastrointestinal basidiobolomycosis using voriconazole mono-therapy. In addition, we present extensive review of pediatric gastrointestinal basidiobolomycosis in medical literature.

摘要

蛙粪霉病是一种由蛙粪霉引起的罕见真菌感染。绝大多数胃肠道蛙粪霉病病例报告于热带和亚热带地区。我们报告了一名沙特儿科患者,患有回肠蛙粪霉病,最初临床表现类似急性阑尾炎,后被误诊为克罗恩病。我们的病例是首例报道使用伏立康唑单药治疗小儿胃肠道蛙粪霉病有效的病例。此外,我们还对医学文献中关于小儿胃肠道蛙粪霉病的内容进行了广泛综述。

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