Lau Christopher, Killian Keith J, Samuels Yardena, Rudloff Udo
Clinical Genetics Branch, Center for Cancer Research, NCI, NIH, Bethesda, MD, USA.
Methods Mol Biol. 2014;1102:461-80. doi: 10.1007/978-1-62703-727-3_24.
Recent sequencing efforts in melanoma have elucidated many previously unknown molecular pathways and biological mechanisms involved in melanoma development and progression and have yielded a number of promising targets for molecular therapy. As sequencing technologies have become more sophisticated and have revealed an ever-increasing complexity of the genetic landscape of melanoma, it has become clear that sequencing methods applied to clinical specimens have to reliably capture not only recurrent "hotspot" mutations like BRAFV600 and NRASQ61 or "mini-hotspot" mutations like exon 11 and 13 c-KIT but also heterogeneous somatic mutations dispersed across multiple functionally conserved regions of genes or entire genes. One such example in melanoma is the ERBB4 receptor, or HER4, a member of the Erb receptor family, which has recently been shown to be a major oncogenic "driver" in melanoma. Mutated ERBB4 signaling activates both aberrant ERBB4 and PI3K-AKT signal transduction, mediates sensitivity to small-molecule inhibition with the dual-tyrosine kinase inhibitor lapatinib, and has recently also been implied in oncogenic glutamatergic signaling in melanoma. Mutations involving the ERBB4 gene act as "gain-of-function" mutations and predominantly involve the extracellular domains of the receptor. Additional sequencing efforts have recently identified recurrent mutations ("mini-hotspots") or mutation clusters which affect the regulation of, e.g., ligand binding, arrangement of extracellular domain alignment, or intramolecular tether formation.In this chapter, we describe the methods used to determine the mutation status of all exons of the ERBB4 gene in clinical specimens obtained from patients afflicted by metastatic melanoma. Upon slight modifications, this protocol can also be used for mutational analysis of other oncogenes affected by "non-hotspot" mutations dispersed across multiple exons. This sequencing technique has successfully been applied within a clinical trial selecting patients with ERBB4-mutant melanoma for lapatinib treatment. With the increasing emergence of low-frequency oncogenes affected by heterogeneous activating mutations located in different exons and regions this method will provide a mean to translate the promise of recently obtained genetic knowledge into clinical genotype-directed targeted therapy trials.
近期针对黑色素瘤的测序工作阐明了许多此前未知的、参与黑色素瘤发生发展的分子途径和生物学机制,并产生了一些有前景的分子治疗靶点。随着测序技术变得更加成熟,黑色素瘤基因图谱的复杂性也日益凸显,很明显,应用于临床标本的测序方法不仅要可靠地捕获BRAFV600和NRASQ61等常见的“热点”突变,或外显子11和13的c-KIT等“微热点”突变,还要捕获分散在基因多个功能保守区域或整个基因中的异质性体细胞突变。黑色素瘤中的一个例子是ERBB4受体,即HER4,它是Erb受体家族的成员,最近被证明是黑色素瘤中的一个主要致癌“驱动因素”。突变的ERBB4信号激活异常的ERBB4和PI3K-AKT信号转导,介导对双酪氨酸激酶抑制剂拉帕替尼的小分子抑制的敏感性,最近还被认为与黑色素瘤中的致癌性谷氨酸能信号有关。涉及ERBB4基因的突变作为“功能获得性”突变,主要涉及受体的细胞外结构域。最近的其他测序工作已经确定了影响例如配体结合、细胞外结构域排列或分子内连接形成调控的复发性突变(“微热点”)或突变簇。在本章中,我们描述了用于确定从转移性黑色素瘤患者获得的临床标本中ERBB4基因所有外显子突变状态的方法。稍作修改后,该方案也可用于受分散在多个外显子中的“非热点”突变影响的其他癌基因的突变分析。这种测序技术已成功应用于一项临床试验,该试验选择ERBB4突变型黑色素瘤患者进行拉帕替尼治疗。随着受位于不同外显子和区域的异质性激活突变影响的低频癌基因的不断出现,这种方法将为把最近获得的基因知识转化为临床基因型导向的靶向治疗试验提供一种手段。