Chiocchetti Andreas G, Bour Hanna S, Freitag Christine M
Department of Child and Adolescent Psychiatry, Psychosomatics and Psychotherapy, University Hospital Frankfurt, Goethe University, Deutschordenstraße 50, 60528, Frankfurt am Main, Germany,
J Neural Transm (Vienna). 2014 Sep;121(9):1081-106. doi: 10.1007/s00702-014-1161-y. Epub 2014 Feb 4.
Autism spectrum disorders (ASD) are neurodevelopmental disorders with early onset in childhood. Most of the risk for ASD can be explained by genetic variants that act in interaction with biological environmental risk factors. However, the architecture of the genetic components is still unclear. Genetic studies and subsequent systems biological approaches described converging functional effects of identified genes towards pathways relevant for neuronal signalling. Mouse models suggest an aberrant synaptic plasticity at the neuropathological level, which is believed to be conferred by dysregulation of long-term potentiation or depression of neuronal connections. A central pathway regulating these mechanisms is glutamatergic signalling. Here, we hypothesized that susceptibility genes for ASD are enriched for components of this pathway. To further understand the impact of ASD risk genes on the glutamatergic pathway, we performed a systematic review using the literature database "pubmed" and the "AutismKB" knowledgebase. We provide an overview of the glutamatergic system in typical brain function and development, and summarize findings from linkage, association, copy number variants, and sequencing studies in ASD to provide a comprehensive picture of the glutamatergic landscape of ASD genetics. Genetic variants associated with ASD were enriched in glutamatergic pathways, affecting receptor signalling, metabolism and transport. Furthermore, in genetically modified mouse models for ASD, pharmacological compounds acting on ionotropic or metabotropic receptor activity are able to rescue ASD reminscent phenotypes. We conclude that glutamatergic genetic risk factors for ASD show a complex pattern and further studies are needed to fully understand its mechanisms, before translation of findings into clinical applications and individualized treatment approaches will be possible.
自闭症谱系障碍(ASD)是一种在儿童早期发病的神经发育障碍。ASD的大多数风险可由与生物环境风险因素相互作用的基因变异来解释。然而,遗传成分的结构仍不清楚。已开展的基因研究及后续的系统生物学方法表明,已鉴定出的基因对与神经元信号传导相关的通路具有趋同的功能影响。小鼠模型显示在神经病理学水平存在异常的突触可塑性,这被认为是由神经元连接的长时程增强或抑制失调所致。调节这些机制的一条核心通路是谷氨酸能信号传导。在此,我们假设ASD的易感基因富含该通路的成分。为了进一步了解ASD风险基因对谷氨酸能通路的影响,我们使用文献数据库“pubmed”和“AutismKB”知识库进行了系统综述。我们概述了谷氨酸能系统在典型脑功能和发育中的情况,并总结了ASD连锁、关联、拷贝数变异和测序研究的结果,以全面呈现ASD遗传学的谷氨酸能格局。与ASD相关的基因变异在谷氨酸能通路中富集,影响受体信号传导、代谢和转运。此外,在针对ASD的基因改造小鼠模型中,作用于离子型或代谢型受体活性的药理化合物能够挽救ASD相关的表型。我们得出结论,ASD的谷氨酸能遗传风险因素呈现出复杂的模式,在将研究结果转化为临床应用和个体化治疗方法之前,还需要进一步研究以充分了解其机制。