Guo Zhi-Ping, Yang Lin-Hua, Chen Jian-Fang, Chen Xiu-Hua, Zhang Yao-Fang
Department of Hematology, The Second Hospital of Shanxi Medical University, No. 382, WuYi Rd., Taiyuan, 030001 Shanxi People's Republic of China.
Indian J Hematol Blood Transfus. 2014 Sep;30(Suppl 1):162-5. doi: 10.1007/s12288-013-0310-z. Epub 2014 Jan 8.
In the present case study, a 42-year-old Chinese woman fulfilling the WHO criteria for idiopathic hypereosinophilic syndrome (IHES) who exhibited clinical manifestations of eosinophilic infiltration of multiple tissues including the lungs, heart, central and peripheral nervous system, gastrointestinal tract, spleen, liver and unexplained clinical findings is described. Laboratory investigations revealed the topmost white blood cell and eosinophil that were 150 × 10(9)/L and 136 × 10(9)/L (90.6 %), respectively. To our knowledge, such a large number of eosinophils has rarely been reported, and all reactive causes of hypereosinophilia were excluded. Treatment with cytotoxic chemotherapy, prednisone and dexamethasone was not beneficial. The patient showed a remarkable hematological response when methylprednisolone pulse therapy was initiated when progression of respiratory symptoms occurred, but without clinical remission. The patient subsequently died. We consider that her critical organ damage and poor prognosis were related to the large number of eosinophils and delayed effective anti-eosinophilic therapy after severe organ damage occurred. This case highlights the clinical importance of methylprednisolone pulse therapy which should be initiated without delay once the diagnosis of IHES is made.
在本病例研究中,描述了一名42岁的中国女性,她符合世界卫生组织特发性高嗜酸性粒细胞综合征(IHES)的标准,表现出多种组织嗜酸性粒细胞浸润的临床表现,包括肺、心脏、中枢和周围神经系统、胃肠道、脾脏、肝脏以及不明原因的临床发现。实验室检查显示白细胞计数最高达150×10⁹/L,嗜酸性粒细胞计数为136×10⁹/L(90.6%)。据我们所知,如此大量的嗜酸性粒细胞鲜有报道,且排除了所有引起嗜酸性粒细胞增多的反应性病因。细胞毒性化疗、泼尼松和地塞米松治疗均无效。当出现呼吸道症状进展时开始甲泼尼龙冲击治疗,患者出现了显著的血液学反应,但未实现临床缓解。患者随后死亡。我们认为,她的重要器官损害和预后不良与大量嗜酸性粒细胞以及严重器官损害发生后延迟有效的抗嗜酸性粒细胞治疗有关。该病例凸显了甲泼尼龙冲击治疗的临床重要性,一旦确诊IHES应立即开始治疗,不得延误。