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睡眠起始时出现的腹部不安和类似脊髓固有肌阵挛:一种不寻常的重叠综合征。

A restless abdomen and propriospinal myoclonus like at sleep onset: an unusual overlap syndrome.

作者信息

Baiardi Simone, La Morgia Chiara, Mondini Susanna, Cirignotta Fabio

机构信息

Department of Biomedical and Neuromotor Sciences, University of Bologna, Neurology Unit, S. Orsola-Malpighi Hospital, AOU Bologna, Italy.

出版信息

BMJ Case Rep. 2015 Mar 27;2015:bcr2014206679. doi: 10.1136/bcr-2014-206679.

DOI:10.1136/bcr-2014-206679
PMID:25820108
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC4386442/
Abstract

We report for the first time the association between restless abdomen, a phenotypic variant of restless legs syndrome in which symptoms are limited to the abdomen, and propriospinal myoclonus at sleep onset causing severe insomnia. The treatment with a low-dosage of dopaminergic drug (pramipexole) induced the immediate disappearance of both symptoms, which was documented by video-polysomnography.

摘要

我们首次报告了不安腹部(不安腿综合征的一种表型变异,其症状仅限于腹部)与入睡时脊髓性肌阵挛导致严重失眠之间的关联。低剂量多巴胺能药物(普拉克索)治疗使两种症状立即消失,这通过视频多导睡眠图得到了证实。

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本文引用的文献

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Propriospinal myoclonus: clinical reappraisal and review of literature.脊髓性肌阵挛:临床重新评估及文献综述
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Psychogenic axial myoclonus: clinical features and long-term outcome.心因性轴索性肌阵挛:临床特征与长期预后
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Restless abdomen: a phenotypic variant of restless legs syndrome.不安腹部:不安腿综合征的一种表型变异。
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Propriospinal myoclonus at sleep onset.睡眠起始时的脊髓性肌阵挛
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Propriospinal myoclonus: a motor phenomenon found in restless legs syndrome different from periodic limb movements during sleep.脊髓性肌阵挛:一种在不宁腿综合征中发现的运动现象,不同于睡眠期周期性肢体运动。
Mov Disord. 2005 Oct;20(10):1323-9. doi: 10.1002/mds.20599.
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Propriospinal myoclonus at the sleep-wake transition: a new type of parasomnia.睡眠-觉醒转换期的脊髓固有肌阵挛:一种新型的异态睡眠。
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Propriospinal myoclonus upon relaxation and drowsiness: a cause of severe insomnia.放松及困倦时的脊髓固有肌阵挛:严重失眠的一个原因
Mov Disord. 1997 Jan;12(1):66-72. doi: 10.1002/mds.870120112.