Ojha Vineeta, Samui Partha P, Dakshit Debashis
Department of Radiodiagnosis, Medical College Kolkata, 88, College Street, Kolkata 700073, West Bengal, India.
Respir Med Case Rep. 2015 May 22;16:24-8. doi: 10.1016/j.rmcr.2015.02.011. eCollection 2015.
Intralobar pulmonary sequestration is a rare congenital malformation characterized by the presence of nonfunctional parenchymal lung tissue, receiving systemic arterial blood supply and lacking normal communication with tracheobronchial tree. Recurrent pneumonia and massive hemoptysis are life threatening complications associated with it. Delay in the diagnosis and management can be fatal. We report here a case of intralobar pulmonary sequestration in a 18 year old female who presented with recurrent severe episodes of pneumonia and hemoptysis forcing her to drop out of school. The diagnosis was confirmed by CECT Thorax and CT Angiography. The patient was managed by minimally invasive endovascular treatment in the form of feeding artery embolization. She made a full recovery with satisfactory outcome. On subsequent follow up, there was no recurrence of symptoms and she is doing well socially and academically. The aim of this case report is to show feasibility and safety of embolization as a less-invasive management option for adult pulmonary sequestration complicated with hemoptysis and LRTIs and emphasize the importance of such minimally invasive technique to enhance the quality of life in such patients.
叶内型肺隔离症是一种罕见的先天性畸形，其特征是存在无功能的肺实质组织，接受体循环动脉血供，且与气管支气管树无正常连通。反复肺炎和大量咯血是与之相关的危及生命的并发症。诊断和治疗的延迟可能是致命的。我们在此报告一例18岁女性叶内型肺隔离症病例，该患者反复出现严重的肺炎和咯血发作，被迫辍学。胸部CT血管造影和CT血管成像确诊了该疾病。患者接受了以供血动脉栓塞形式的微创血管内治疗。她完全康复，结果令人满意。在随后的随访中，症状未复发，她在社交和学业方面表现良好。本病例报告的目的是展示栓塞作为成人肺隔离症合并咯血和下呼吸道感染的一种侵入性较小的管理选择的可行性和安全性，并强调这种微创技术对提高此类患者生活质量的重要性。
