Livraghi-Butrico Alessandra, Grubb Barbara R, Wilkinson Kristen J, Volmer Allison S, Burns Kimberly A, Evans Christopher M, O'Neal Wanda K, Boucher Richard C
University of North Carolina Marsico Lung Institute/ Cystic Fibrosis Center, School of Medicine, The University of North Carolina at Chapel Hill, 125 Mason Farm Rd. 27599, Chapel Hill, NC, USA.
Department of Medicine, University of Colorado School of Medicine, 12700 E 19th Avenue, Mailstop 8611, Research Complex 2, Room 3121, Aurora, Colorado 80045, USA.
Mucosal Immunol. 2017 Mar;10(2):395-407. doi: 10.1038/mi.2016.63. Epub 2016 Jul 20.
Airway diseases, including cigarette smoke-induced chronic bronchitis, cystic fibrosis, and primary ciliary dyskinesia are associated with decreased mucociliary clearance (MCC). However, it is not known whether a simple reduction in MCC or concentration-dependent mucus adhesion to airway surfaces dominates disease pathogenesis or whether decreasing the concentration of secreted mucins may be therapeutic. To address these questions, Scnn1b-Tg mice, which exhibit airway mucus dehydration/adhesion, were compared and crossed with Muc5b- and Muc5ac-deficient mice. Absence of Muc5b caused a 90% reduction in MCC, whereas Scnn1b-Tg mice exhibited an ∼50% reduction. However, the degree of MCC reduction did not correlate with bronchitic airway pathology, which was observed only in Scnn1b-Tg mice. Ablation of Muc5b significantly reduced the extent of mucus plugging in Scnn1b-Tg mice. However, complete absence of Muc5b in Scnn1b-Tg mice was associated with increased airway inflammation, suggesting that Muc5b is required to maintain immune homeostasis. Loss of Muc5ac had few phenotypic consequences in Scnn1b-Tg mice. These data suggest that: (i) mucus hyperconcentration dominates over MCC reduction alone to produce bronchitic airway pathology; (ii) Muc5b is the dominant contributor to the Scnn1b-Tg phenotype; and (iii) therapies that limit mucin secretion may reduce plugging, but complete Muc5b removal from airway surfaces may be detrimental.
气道疾病,包括香烟烟雾诱导的慢性支气管炎、囊性纤维化和原发性纤毛运动障碍,都与黏液纤毛清除功能(MCC)下降有关。然而,目前尚不清楚单纯的MCC降低或浓度依赖性的黏液与气道表面的黏附在疾病发病机制中哪个起主导作用,也不清楚降低分泌性黏蛋白的浓度是否具有治疗作用。为了解决这些问题,对表现出气道黏液脱水/黏附的Scnn1b-Tg小鼠进行了比较,并与Muc5b和Muc5ac缺陷小鼠进行了杂交。缺乏Muc5b导致MCC降低90%,而Scnn1b-Tg小鼠的MCC降低约50%。然而,MCC降低的程度与支气管炎性气道病理变化并不相关,后者仅在Scnn1b-Tg小鼠中观察到。敲除Muc5b显著降低了Scnn1b-Tg小鼠的黏液堵塞程度。然而,Scnn1b-Tg小鼠中完全缺乏Muc5b与气道炎症增加有关,这表明Muc5b是维持免疫稳态所必需的。在Scnn1b-Tg小鼠中,Muc5ac的缺失几乎没有表型后果。这些数据表明:(i)黏液高浓度在导致支气管炎性气道病理变化方面比单纯的MCC降低起更主导的作用;(ii)Muc5b是Scnn1b-Tg表型的主要促成因素;(iii)限制黏蛋白分泌的疗法可能会减少堵塞,但从气道表面完全去除Muc5b可能是有害的。