Zhang Qian, Wang Rong, Liu Yaping, Zhang Yan, Wang Shuo, Cao Yong, Zhao Yuanli, Liu Xingju, Wang Jia, Deng Xiaofeng, Gao Faliang, Yang Ziwen, Zhao Meng, Ge Peicong, Ma Yonggang, Zhao Jizong, Zhang Dong
Department of Neurosurgery, Beijing Tiantan Hospital, Capital Medical University, Beijing, China; China National Clinical Research Center for Neurological Diseases, Beijing, China; Center of Stroke, Beijing Institute for Brain Disorders, Beijing, China; Beijing Key Laboratory of Translational Medicine for Cerebrovascular Disease, Beijing, China.
McKusick-Zhang Center for Genetic Medicine, State Key Laboratory of Medical Molecular Biology, Institute of Basic Medical Sciences, Chinese Academy of Medical Sciences, and Peking Union Medical College, Beijing, China.
World Neurosurg. 2016 Dec;96:474-482. doi: 10.1016/j.wneu.2016.09.018. Epub 2016 Sep 16.
To elucidate the clinical features, risk factors for contralateral progression, and long-term outcomes of patients with unilateral moyamoya disease (MMD).
We retrospectively reviewed 109 patients with unilateral MMD treated at Beijing Tiantan Hospital. Clinical features, radiologic findings, and outcomes were analyzed.
The mean age at diagnosis was 30.8 ± 14.2 years with a one-peak distribution in the thirties. The ratio of women to men was 1.1:1. Familial occurrence was 5.5%. The primary symptoms at initial presentation were transient ischemic attack (39.4%), infarction (22%), and hemorrhage (26.6%). The distribution of the initial Suzuki stage was as follows: stage 2, n = 33; stage 3, n = 35; stage 4, n = 27; stage 5, n = 11, and stage 6, n = 3. Contralateral abnormality on initial angiography occurred in 19 adult patients (17.4%). Posterior cerebral artery involvement was observed in 28 (25.7%) patients. During the average follow-up of 43.8 ± 21.3 months, contralateral progression was observed in 18 patients (16.5%). Contralateral abnormalities (P = 0.033) on initial angiography and infarction at initial presentation (P = 0.041) were significantly associated with contralateral progression in adults and children, respectively. Approximately 91.7% of patients had a modified Rankin Scale score of 0-2 during follow-up.
A one-peak pattern in age distribution, lower grade of Suzuki stage, fewer familial cases, and posterior cerebral artery involvement were observed in patients with unilateral MMD. Contralateral abnormalities on initial angiography and infarction at onset were risk factors for contralateral progression in adult and pediatric patients, respectively. Good functional outcomes can be anticipated in the vast majority of surgically treated patients.
阐明单侧烟雾病(MMD)患者的临床特征、对侧进展的危险因素及长期预后。
我们回顾性分析了在北京天坛医院接受治疗的109例单侧MMD患者。对其临床特征、影像学表现及预后进行了分析。
诊断时的平均年龄为30.8±14.2岁,呈三十多岁的单峰分布。女性与男性的比例为1.1:1。家族性发病占5.5%。初次就诊时的主要症状为短暂性脑缺血发作(39.4%)、梗死(22%)和出血(26.6%)。初次铃木分期分布如下:2期,n = 33;3期,n = 35;4期,n = 27;5期,n = 11;6期,n = 3。初次血管造影时对侧异常在19例成年患者中出现(17.4%)。28例(25.7%)患者观察到大脑后动脉受累。在平均43.8±21.3个月的随访期间,18例患者(16.5%)出现对侧进展。初次血管造影时的对侧异常(P = 0.033)和初次就诊时的梗死(P = 0.041)分别与成人和儿童的对侧进展显著相关。随访期间约91.7%的患者改良Rankin量表评分为0 - 2分。
单侧MMD患者年龄分布呈单峰模式、铃木分期较低、家族性病例较少且大脑后动脉受累。初次血管造影时的对侧异常和发病时的梗死分别是成年和儿童患者对侧进展的危险因素。绝大多数接受手术治疗的患者可预期良好的功能预后。