Wang Steven, Yan Jie, Zhou Guangde, Heintzelman Rebecca, Hou J Steve
Department of Pathology and Laboratory Medicine, Drexel University College of Medicine, 245 N. 15th Street, MS 435, Philadelphia, PA 19102, USA.
Case Rep Hematol. 2016;2016:6054017. doi: 10.1155/2016/6054017. Epub 2016 Sep 26.
Myeloproliferative neoplasms (MPNs) are hematopoietic malignancies characterized by unchecked proliferation of differentiated myeloid cells. The most common BCR-ABL1-negative MPNs are polycythemia vera, essential thrombocythemia, and primary myelofibrosis. The discovery of JAK2 V617F mutation has improved our understanding of the molecular basis of MPN. The high frequency of JAK2 mutation in MPN makes JAK2 mutation testing an essential diagnostic tool and potential therapeutic target for MPN. Here, we present a rare case of a 34-year-old patient who was initially diagnosed with acute myeloid leukemia (AML) with mutated NPM1. After chemotherapy treatment followed by granulocyte colony stimulating factor administration, the patient achieved complete remission of AML. However, the bone marrow showed hypercellularity with granulocytic hyperplasia, markedly increased atypical megakaryocytes (50.2/HPF) with focal clustering, and reticulin fibrosis (3/4). JAK2 V617F mutation was also detected. Considering the possibility of AML transformed from a previous undiagnosed MPN, patient underwent peripheral blood allogenic stem cell transplant. This case illustrates the diagnostic challenges of firmly establishing a diagnosis between similar, but distinct, disease entities and an accurate clinicopathological differentiation is crucial.
骨髓增殖性肿瘤(MPN)是一种造血系统恶性肿瘤,其特征是分化的髓系细胞不受控制地增殖。最常见的BCR-ABL1阴性MPN是真性红细胞增多症、原发性血小板增多症和原发性骨髓纤维化。JAK2 V617F突变的发现增进了我们对MPN分子基础的理解。MPN中JAK2突变的高频率使得JAK2突变检测成为MPN的重要诊断工具和潜在治疗靶点。在此,我们报告一例罕见病例,一名34岁患者最初被诊断为伴有NPM1突变的急性髓系白血病(AML)。经过化疗并给予粒细胞集落刺激因子后,患者的AML达到完全缓解。然而,骨髓显示细胞增多,伴有粒细胞增生,非典型巨核细胞明显增多(50.2/HPF)且有局灶性聚集,以及网状纤维纤维化(3/4)。还检测到JAK2 V617F突变。考虑到AML可能由先前未诊断的MPN转化而来,患者接受了外周血异基因干细胞移植。该病例说明了在相似但不同的疾病实体之间准确建立诊断的诊断挑战,准确的临床病理鉴别至关重要。