Sharma Tara L, Yeaney Gabrielle A, Soltanzadeh Payam, Li Yuebing, Cotta Claudiu V
Neurology Institute, Robert J. Tomsich Pathology and Laboratory Medicine Institute, Cleveland Clinic, Cleveland, Ohio, USA.
Pathology, Robert J. Tomsich Pathology and Laboratory Medicine Institute, Cleveland Clinic, Cleveland, Ohio, USA.
Neuropathology. 2017 Aug;37(4):365-370. doi: 10.1111/neup.12376. Epub 2017 Mar 20.
Intravascular T-cell lymphomas are rare, poorly characterized lesions. We discuss the clinical, radiologic and especially the laboratory characteristics of a lesion which presented in a 62-year-old woman with a history of progressive CNS abnormalities. Throughout the course of the disease, radiologic findings consisted mainly of multifocal mixed areas of ischemia and vasogenic edema involving cortical and subcortical regions. A brain biopsy identified an abnormal T-cell population confined to lumens of vessels. These T-cells were abnormal cytotoxic cells, positive for CD3, CD8, and negative for CD2, CD4, CD5, CD7 and CD30. While flow cytometry and immunohistochemistry failed to identify a similar population in the blood or bone marrow, molecular studies showed a clonal T-cell population in both the brain and the bone marrow. No other organs were involved. In spite of aggressive treatment, the patient's medical condition continued to progress and she passed away. In conclusion, this abnormal population of cytotoxic T-cells with intravascular localization probably represents a specific type of T-cell lymphoma with specific clinical, radiologic, molecular and immunophenotypic characteristics.
血管内T细胞淋巴瘤是罕见的、特征描述不清的病变。我们讨论了一名62岁有进行性中枢神经系统异常病史女性患者所患病变的临床、放射学尤其是实验室特征。在疾病过程中,放射学表现主要为累及皮质和皮质下区域的多灶性缺血和血管源性水肿混合区。脑活检发现异常T细胞群体局限于血管腔内。这些T细胞是异常的细胞毒性细胞,CD3、CD8呈阳性,CD2、CD4、CD5、CD7和CD30呈阴性。虽然流式细胞术和免疫组化未能在血液或骨髓中鉴定出类似群体,但分子研究显示脑和骨髓中均存在克隆性T细胞群体。无其他器官受累。尽管进行了积极治疗,患者病情仍持续进展并最终死亡。总之,这种具有血管内定位的异常细胞毒性T细胞群体可能代表了一种具有特定临床、放射学、分子和免疫表型特征的特殊类型T细胞淋巴瘤。