Hulverson Matthew A, Vinayak Sumiti, Choi Ryan, Schaefer Deborah A, Castellanos-Gonzalez Alejandro, Vidadala Rama S R, Brooks Carrie F, Herbert Gillian T, Betzer Dana P, Whitman Grant R, Sparks Hayley N, Arnold Samuel L M, Rivas Kasey L, Barrett Lynn K, White A Clinton, Maly Dustin J, Riggs Michael W, Striepen Boris, Van Voorhis Wesley C, Ojo Kayode K
Division of Allergy & Infectious Disease, Center for Emerging & Reemerging Infectious Disease (CERID), University of Washington, Seattle, Washington 98109, USA.
Center for Tropical and Emerging Global Diseases, University of Georgia, Athens, Georgia 30602, USA
J Infect Dis. 2017 Apr 15;215(8):1275-1284. doi: 10.1093/infdis/jix120.
Bumped kinase inhibitors (BKIs) of Cryptosporidium parvum calcium-dependent protein kinase 1 (CpCDPK1) are leading candidates for treatment of cryptosporidiosis-associated diarrhea. Potential cardiotoxicity related to anti-human ether-à-go-go potassium channel (hERG) activity of the first-generation anti-Cryptosporidium BKIs triggered further testing for efficacy. A luminescence assay adapted for high-throughput screening was used to measure inhibitory activities of BKIs against C. parvum in vitro. Furthermore, neonatal and interferon γ knockout mouse models of C. parvum infection identified BKIs with in vivo activity. Additional iterative experiments for optimum dosing and selecting BKIs with minimum levels of hERG activity and frequencies of other safety liabilities included those that investigated mammalian cell cytotoxicity, C. parvum proliferation inhibition in vitro, anti-human Src inhibition, hERG activity, in vivo pharmacokinetic data, and efficacy in other mouse models. Findings of this study suggest that fecal concentrations greater than parasite inhibitory concentrations correlate best with effective therapy in the mouse model of cryptosporidiosis, but a more refined model for efficacy is needed.
微小隐孢子虫钙依赖性蛋白激酶1(CpCDPK1)的碰撞激酶抑制剂(BKIs)是治疗隐孢子虫病相关性腹泻的主要候选药物。第一代抗隐孢子虫BKIs与抗人醚 - 去极化钾通道(hERG)活性相关的潜在心脏毒性引发了进一步的疗效测试。一种适用于高通量筛选的发光测定法用于测量BKIs在体外对微小隐孢子虫的抑制活性。此外,微小隐孢子虫感染的新生小鼠和干扰素γ基因敲除小鼠模型确定了具有体内活性的BKIs。为了确定最佳剂量并选择具有最低hERG活性水平和其他安全风险频率的BKIs而进行的额外迭代实验包括那些研究哺乳动物细胞毒性、体外微小隐孢子虫增殖抑制、抗人Src抑制、hERG活性、体内药代动力学数据以及在其他小鼠模型中的疗效的实验。本研究结果表明,在隐孢子虫病小鼠模型中,粪便浓度大于寄生虫抑制浓度与有效治疗的相关性最佳,但需要一个更精确的疗效模型。