Department of Translational Medical Sciences, Section of Pediatrics, Federico II University, Via S. Pansini, 5, 80131, Naples, Italy.
J Clin Immunol. 2017 Nov;37(8):751-758. doi: 10.1007/s10875-017-0445-z. Epub 2017 Sep 21.
Since the discovery of FOXN1 deficiency, the human counterpart of the nude mouse, a growing body of evidence investigating the role of FOXN1 in thymus and skin, has been published. FOXN1 has emerged as fundamental for thymus development, function, and homeostasis, representing the master regulator of thymic epithelial and T cell development. In the skin, it also plays a pivotal role in keratinocytes and hair follicle cell differentiation, although the underlying molecular mechanisms still remain to be fully elucidated. The nude severe combined immunodeficiency phenotype is indeed characterized by the clinical hallmarks of athymia with severe T cell immunodeficiency, congenital alopecia, and nail dystrophy. In this review, we summarize recent discoveries in the field and give interesting perspective about new and promising therapeutic approaches for disorders of immune system with athymia.
自 FOXN1 缺陷(裸鼠的人类对应物)被发现以来,越来越多的研究FOXN1 在胸腺和皮肤中的作用的证据已经发表。FOXN1 已成为胸腺发育、功能和内稳态的基础,是胸腺上皮细胞和 T 细胞发育的主要调节剂。在皮肤中,它在角质形成细胞和毛囊细胞分化中也起着关键作用,尽管其潜在的分子机制仍有待充分阐明。裸鼠严重联合免疫缺陷表型的临床特征确实是无胸腺伴严重 T 细胞免疫缺陷、先天性脱发和指甲发育不良。在这篇综述中,我们总结了该领域的最新发现,并对无胸腺免疫紊乱的新的有前途的治疗方法提供了有趣的观点。