Liu Dekang, Frederiksen Jane H, Liberti Sascha E, Lützen Anne, Keijzers Guido, Pena-Diaz Javier, Rasmussen Lene Juel
Center for Healthy Aging, University of Copenhagen, Denmark.
Department of Cellular and Molecular Medicine, University of Copenhagen, Denmark.
Nucleic Acids Res. 2017 Sep 19;45(16):9427-9440. doi: 10.1093/nar/gkx611.
DNA mismatch repair (MMR) is a highly-conserved DNA repair mechanism, whose primary role is to remove DNA replication errors preventing them from manifesting as mutations, thereby increasing the overall genome stability. Defects in MMR are associated with increased cancer risk in humans and other organisms. Here, we characterize the interaction between MMR and a proofreading-deficient allele of the human replicative DNA polymerase delta, PolδD316A;E318A, which has a higher capacity for strand displacement DNA synthesis than wild type Polδ. Human cell lines overexpressing PolδD316A;E318A display a mild mutator phenotype, while nuclear extracts of these cells exhibit reduced MMR activity in vitro, and these defects are complemented by overexpression or addition of exogenous human Exonuclease 1 (EXO1). By contrast, another proofreading-deficient mutant, PolδD515V, which has a weaker strand displacement activity, does not decrease the MMR activity as significantly as PolδD316A;E318A. In addition, PolδD515V does not increase the mutation frequency in MMR-proficient cells. Based on our findings, we propose that the proofreading activity restricts the strand displacement activity of Polδ in MMR. This contributes to maintain the nicks required for EXO1 entry, and in this manner ensures the dominance of the EXO1-dependent MMR pathway.
DNA错配修复(MMR)是一种高度保守的DNA修复机制,其主要作用是消除DNA复制错误,防止这些错误表现为突变,从而提高整体基因组稳定性。MMR缺陷与人类和其他生物体中癌症风险增加有关。在此,我们描述了MMR与人类复制性DNA聚合酶δ的校对缺陷等位基因PolδD316A;E318A之间的相互作用,该等位基因比野生型Polδ具有更高的链置换DNA合成能力。过表达PolδD316A;E318A的人类细胞系表现出轻度的突变表型,而这些细胞的核提取物在体外表现出降低的MMR活性,并且这些缺陷通过过表达或添加外源性人类核酸外切酶1(EXO1)得到补充。相比之下,另一个校对缺陷突变体PolδD515V,其链置换活性较弱,不会像PolδD316A;E318A那样显著降低MMR活性。此外,PolδD515V不会增加MMR功能正常的细胞中的突变频率。基于我们的发现,我们提出校对活性限制了MMR中Polδ的链置换活性。这有助于维持EXO1进入所需的切口,并以此方式确保EXO1依赖性MMR途径的主导地位。