Suppr超能文献

探索在囊性纤维化人群携带者筛查后促进遗传风险信息家庭沟通的方法。

Exploring approaches to facilitate family communication of genetic risk information after cystic fibrosis population carrier screening.

作者信息

Gorrie Anita, Archibald Alison D, Ioannou Liane, Curnow Lisette, McClaren Belinda

机构信息

Department of Paediatrics, The University of Melbourne, Melbourne, VIC, Australia.

Murdoch Children's Research Institute, The Royal Children's Hospital, Melbourne, VIC, Australia.

出版信息

J Community Genet. 2018 Jan;9(1):71-80. doi: 10.1007/s12687-017-0337-1. Epub 2017 Oct 2.

Abstract

Population carrier screening for cystic fibrosis (CF) enables individuals with no known family history of the condition to ascertain their risk of having a child with CF. When an individual is identified as a carrier of CF, a life-shortening condition, they are encouraged to inform their relatives who are at increased risk of being a carrier. Research suggests that the uptake of CF carrier testing amongst relatives of carriers or people with CF is low. This study aimed to explore approaches to facilitate the process of family communication of genetic information after an individual is identified as a carrier of CF through population screening. Five key informants were interviewed to inform the development of a telephone survey which was administered to 21 individuals identified as carriers of CF through population carrier screening at Victorian Clinical Genetics Services. This study suggests that providing carriers with additional information and follow-up support would be appreciated by carriers and could result in more accurate information being disseminated more widely within families, which could lead to more at-risk relatives accessing testing. Suggested strategies to enhance current practice include mailing a fact sheet to carriers and a follow-up telephone call provided by a genetic counsellor to carriers to offer further support in communicating this information to their relatives.

摘要

对囊性纤维化(CF)进行人群携带者筛查,可使无该病家族病史的个体确定自己生育患CF孩子的风险。当个体被确定为CF携带者(一种会缩短寿命的疾病)时,会鼓励他们告知那些成为携带者风险增加的亲属。研究表明,在CF携带者或CF患者的亲属中,CF携带者检测的接受率较低。本研究旨在探索在个体通过人群筛查被确定为CF携带者后,促进遗传信息家庭沟通的方法。对五位关键信息提供者进行了访谈,以指导电话调查的开展,该调查针对在维多利亚临床遗传学服务机构通过人群携带者筛查被确定为CF携带者的21名个体进行。本研究表明,为携带者提供额外信息和后续支持会受到携带者的欢迎,并可能使更准确的信息在家庭中更广泛地传播,从而使更多有风险的亲属能够接受检测。加强当前做法的建议策略包括向携带者邮寄情况说明书,以及由遗传咨询师给携带者打跟进电话,以便在向其亲属传达此信息方面提供进一步支持。

相似文献

4
Cystic fibrosis carrier screening in a high-risk population. Participation based on a traditional recruitment process.
Arch Pediatr Adolesc Med. 1994 Jun;148(6):632-7. doi: 10.1001/archpedi.1994.02170060086017.
5
Effect of family history on disclosure patterns of cystic fibrosis carrier status.
Am J Med Genet C Semin Med Genet. 2003 May 15;119C(1):70-7. doi: 10.1002/ajmg.c.10008.
9
Population-based genetic screening for cystic fibrosis: attitudes and outcomes.
Public Health Genomics. 2010;13(7-8):449-56. doi: 10.1159/000276544. Epub 2010 Jan 14.

引用本文的文献

1
Addressing family communication in genetic counseling: A scoping review of process studies.
J Genet Couns. 2025 Aug;34(4):e70067. doi: 10.1002/jgc4.70067.
2
Factors Influencing Patient Disclosure of Parkinson's Disease Genetic Testing Results to Relatives.
Mov Disord Clin Pract. 2024 Jul;11(7):786-794. doi: 10.1002/mdc3.14043. Epub 2024 Apr 8.
3
Interventions to support patients with sharing genetic test results with at-risk relatives: a synthesis without meta-analysis (SWiM).
Eur J Hum Genet. 2023 Sep;31(9):988-1002. doi: 10.1038/s41431-023-01400-1. Epub 2023 Jun 21.
4
Experiences of nonpregnant couples after receiving reproductive genetic carrier screening results in Belgium.
Eur J Hum Genet. 2023 Jun;31(6):696-702. doi: 10.1038/s41431-023-01310-2. Epub 2023 Feb 15.
5
Summary of the experiences, knowledge, medical management, and family communication of monoallelic MUTYH carriers.
J Genet Couns. 2023 Apr;32(2):342-350. doi: 10.1002/jgc4.1641. Epub 2022 Oct 17.
8
Evaluation of the template letter regarding the disclosure of genetic information within the family in France.
J Community Genet. 2019 Oct;10(4):489-499. doi: 10.1007/s12687-019-00418-7. Epub 2019 Mar 27.

本文引用的文献

2
Population-based genetic carrier screening for cystic fibrosis in Victoria.
Med J Aust. 2014 Mar 3;200(4):205-6. doi: 10.5694/mja13.10864.
4
Newborn screening for cystic fibrosis.
Curr Opin Pediatr. 2012 Jun;24(3):329-35. doi: 10.1097/MOP.0b013e328353489a.
6
Shock, adjust, decide: reproductive decision making in cystic fibrosis (CF) carrier couples--a qualitative study.
J Genet Couns. 2011 Aug;20(4):404-17. doi: 10.1007/s10897-011-9363-z. Epub 2011 Apr 5.
7
ACOG Committee Opinion No. 486: Update on carrier screening for cystic fibrosis.
Obstet Gynecol. 2011 Apr;117(4):1028-1031. doi: 10.1097/AOG.0b013e31821922c2.
8
A case for cystic fibrosis carrier testing in the general population.
Med J Aust. 2011 Feb 21;194(4):208-9. doi: 10.5694/j.1326-5377.2011.tb03781.x.
9
Emerging issues in cystic fibrosis newborn screening.
Curr Opin Pulm Med. 2010 Nov;16(6):584-90. doi: 10.1097/MCP.0b013e32833e9e27.
10
Uptake of carrier testing in families after cystic fibrosis diagnosis through newborn screening.
Eur J Hum Genet. 2010 Oct;18(10):1084-9. doi: 10.1038/ejhg.2010.78. Epub 2010 May 26.

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验