King Nakesha, Ramesh Shilpa S, Essandoh Michael, Merritt Robert E
Department of Thoracic Surgery, The Ohio State University Wexner Medical Center, Columbus, Ohio.
Department of Anesthesiology, The Ohio State University Wexner Medical Center, Columbus, Ohio.
Ann Thorac Surg. 2017 Nov;104(5):e367-e369. doi: 10.1016/j.athoracsur.2017.06.068.
Congenital lobar emphysema is a rare pulmonary malformation typically diagnosed during infancy and is characterized by bullous disease. A 28-year-old woman, who presented with 1 week of progressive dyspnea and chest pain, was found to have left hemithoracic lung hyperinflation with perfusion deficit upon radiographic evaluation. Bullous disease was found intraoperatively to originate from 1 lower lobe segment. Normal parenchymal lung expansion occurred following resection of the affected segment. Therefore, we present a rare case of congenital lobar emphysema resulting in near-complete occupancy of the left hemithorax and diagnosed in a previously asymptomatic adult without history of predisposing factors.
先天性大叶性肺气肿是一种罕见的肺部畸形,通常在婴儿期被诊断出来,其特征为肺大疱疾病。一名28岁女性,因进行性呼吸困难和胸痛1周前来就诊,经影像学评估发现左半侧胸腔肺过度充气且灌注不足。术中发现肺大疱疾病起源于1个下叶节段。切除受累节段后,肺实质正常扩张。因此,我们报告了一例罕见的先天性大叶性肺气肿病例,该病例导致左半侧胸腔几乎完全被占据,且在一名既往无症状、无易感因素病史的成年人中被诊断出来。