Cummings J F, Wood P A, Walkley S U, de Lahunta A, DeForest M E
Acta Neuropathol. 1985;67(3-4):247-53. doi: 10.1007/BF00687809.
A storage disease in a 2-year-old Japanese Spaniel resembled a GM2 gangliosidosis previously identified in a now extinct line of German Shorthaired Pointers. Despite a later appearance of signs in the Japanese Spaniel, the distribution, staining, and ultrastructure of the stored material were similar in the two breeds. Golgi studies of cerebral cortical neurons revealed the formation of spiny and aspiny enlargements at the axon hillock region (meganeurites) and the growth of secondary neurites from this region. As in the German Shorthaired Pointer model, there was massive storage of GM2 ganglioside as well as a seemingly paradoxical increase in total beta-hexosaminidase activity measured in vitro.
一只2岁的日本猎犬患有一种贮积病,类似于之前在现已灭绝的德国短毛指示犬品系中发现的GM2神经节苷脂沉积症。尽管日本猎犬出现症状的时间较晚,但两个品种中储存物质的分布、染色和超微结构相似。对大脑皮质神经元的高尔基体研究显示,在轴丘区域(巨神经突)形成了有棘和无棘的膨大,并且从该区域长出了次级神经突。与德国短毛指示犬模型一样,存在大量GM2神经节苷脂的储存,以及体外测量的总β-己糖胺酶活性看似矛盾的增加。