Ranasinghe Jagath C, Wickramasinghe Chandani, Rodrigo Ganganath
Department of Pediatrics, Teaching Hospital, Kandy, Sri Lanka.
Department of Radiology, Teaching Hospital, Kandy, Sri Lanka.
BMC Pediatr. 2018 Feb 19;18(1):71. doi: 10.1186/s12887-018-1061-7.
Temporalis muscle hypertrophy is a rare entity of masticatory muscle hypertrophy. All types of masticatory muscle hypertrophies have been documented of which temporalis muscle hypertrophy is one. Temporalis muscle hypertrophy is most commonly bilateral and usually associated with other types of masticatory muscles hypertrophy such as masseter or pterygoid hypertrophy. However, isolated unilateral temporalis muscle hypertrophy is extremely rare and only 9 cases have been reported to date in English literature since 1990 with only two patients less than 18 years. There is no exact etiology identified and the diagnosis is made by muscle biopsy combined with imaging study to exclude other possibilities. Age at presentation is ranges from 15 to 65 years with involvement of both sexes. We report the youngest child who is a seven year old girl with right side isolated unilateral temporalis muscle hypertrophy.
In this patient, we discuss the youngest child with isolated unilateral temporalis muscle hypertrophy and literature review to date. The patient is a seven year old female presenting with painless swelling of the right temporalis muscle. There had no features of inflammation, trauma, neoplasm or history of parafunctions such as bruxism. The child was not complaining significantly headache or visual disturbances as well. She had undergone radiological assessment with ultrasound scan and contrast MRI. The diagnosis was confirmed by muscle biopsy which shows normal muscle architecture. She was managed conservatively with regular follow up.
Isolated unilateral temporalis muscle hypertrophy is extremely rare in children. However this case raises the importance of considering alternative diagnoses despite the condition being rare in the pediatric population.
颞肌肥大是咀嚼肌肥大中一种罕见的情况。已记录了所有类型的咀嚼肌肥大，其中颞肌肥大是其一。颞肌肥大最常见为双侧性，通常与其他类型的咀嚼肌肥大相关，如咬肌或翼状肌肥大。然而，孤立性单侧颞肌肥大极为罕见，自1990年以来，英文文献中仅报道了9例，其中年龄小于18岁的患者仅有2例。目前尚未确定确切病因，诊断需通过肌肉活检并结合影像学检查以排除其他可能性。发病年龄范围为15至65岁，男女均可受累。我们报告了一名最年幼的患者，是一名7岁女孩，患有右侧孤立性单侧颞肌肥大。
在本病例中，我们讨论了最年幼的孤立性单侧颞肌肥大患儿及迄今为止的文献综述。该患者为一名7岁女性，表现为右侧颞肌无痛性肿胀。无炎症、创伤、肿瘤特征或诸如磨牙症等功能异常病史。患儿也无明显头痛或视觉障碍主诉。她接受了超声扫描和增强MRI的影像学评估。肌肉活检显示肌肉结构正常，从而确诊。对她进行了保守治疗并定期随访。
孤立性单侧颞肌肥大在儿童中极为罕见。然而，尽管这种情况在儿科人群中罕见，但该病例凸显了考虑其他诊断的重要性。
