Chen Kuang-Den, Huang Ying-Hsien, Ming-Huey Guo Mindy, Lin Tzu-Yang, Weng Wei-Teng, Yang Hsiang-Jen, Yang Kuender D, Kuo Ho-Chang
Department of Pediatrics and Kawasaki Disease Center, Kaohsiung Chang Gung Memorial Hospital and Chang Gung University College of Medicine, Kaohsiung, Taiwan.
Institute for Translational Research in Biomedicine, Liver Transplantation Center and Department of Surgery, Kaohsiung Chang Gung Memorial Hospital and Chang Gung University College of Medicine, Kaohsiung, Taiwan.
Oncotarget. 2018 Jun 19;9(47):28337-28350. doi: 10.18632/oncotarget.25305.
Kawasaki disease (KD) is a type of acute febrile vasculitis syndrome and is the most frequent cause of cardiac illness in children under the age of five years old. Although the etiology of KD remains largely unknown, some recent genome-wide studies have indicated that epigenetic factors may be important in its pathogenesis. We enrolled 24 KD patients and 24 non-KD controls in this study to access their DNA methylation status using HumanMethylation450 BeadChips. Another 34 KD patients and 62 control subjects were enrolled for expression validation. Of the 3193 CpG methylation regions with a methylation difference ≥ 20% between KD and controls, 3096 CpG loci revealed hypomehtylation, with only 3% being hypermethylated. Pathway buildup identified 11 networked genes among the hypermethylated regions, including four transcription factors: nuclear factor of activated T-cells 1, v-ets avian erythroblastosis virus E26 oncogene homolog 1, runt related transcription factor 3, and retinoic acid receptor gamma, as well as the activator β-catenin. Ten of these network-selected genes demonstrated a significant decrease in mRNA in KD patients, whereas only CTNNB1 significantly decreased in correlation with coronary artery lesions in KD patients. Furthermore, CTNNB1-silenced THP-1 monocytic cells drastically increased the expression of CD40 and significantly increased the expression of both CD40 and CD40L in cocultured human coronary artery endothelial cells. This study is the first to identify network-based susceptible genes of hypermethylated CpG loci, their expression levels, and the functional impact of β-catenin, which may be involved in both the cause and the development of KD.
川崎病(KD)是一种急性发热性血管炎综合征,是五岁以下儿童心脏疾病的最常见病因。尽管KD的病因在很大程度上仍不清楚,但最近的一些全基因组研究表明,表观遗传因素可能在其发病机制中起重要作用。我们在本研究中纳入了24例KD患者和24例非KD对照,使用HumanMethylation450 BeadChips检测他们的DNA甲基化状态。另外纳入了34例KD患者和62例对照进行表达验证。在KD组和对照组之间甲基化差异≥20%的3193个CpG甲基化区域中,3096个CpG位点表现为低甲基化,仅有3%为高甲基化。通路构建在高甲基化区域中鉴定出11个网络连接基因,包括4个转录因子:活化T细胞核因子1、v-ets禽成红细胞增多症病毒E26癌基因同源物1、 runt相关转录因子3和视黄酸受体γ,以及激活剂β-连环蛋白。这些网络选择基因中的10个在KD患者中mRNA显著降低,而只有CTNNB1与KD患者冠状动脉病变相关且显著降低。此外,CTNNB1沉默的THP-1单核细胞显著增加CD40的表达,并在共培养的人冠状动脉内皮细胞中显著增加CD40和CD40L的表达。本研究首次鉴定了基于网络的高甲基化CpG位点易感基因、它们的表达水平以及β-连环蛋白的功能影响,β-连环蛋白可能参与了KD的病因和发展。