Izumi Shintaro, Kimura Kenji, Takeda Yusuke, Tsukamoto Shokichi, Yamazaki Miki, Mishina Tatsuzo, Nagai Yurie, Takaishi Koji, Nagao Yuhei, Oshima-Hasegawa Nagisa, Mitsukawa Shio, Mimura Naoya, Takeuchi Masahiro, Ohwada Chikako, Iseki Tohru, Ota Satoshi, Nakaseko Chiaki, Sakaida Emiko
Department of Hematology, Chiba University Hospital.
Department of Hematology, Chiba Aoba Municipal Hospital.
Rinsho Ketsueki. 2018;59(12):2600-2605. doi: 10.11406/rinketsu.59.2600.
A 60-year-old man with chronic hepatitis C was referred to our hospital with significantly elevated total protein and serum IgM (9,500 mg/dl) levels identified via a routine checkup. Blood examination revealed increased serum IgM-monoclonal protein and serum-soluble IL-2 receptor (sIL2R) levels. Computed tomography and fluorodeoxyglucose positron emission tomography revealed pulmonary masses, abnormal soft tissue masses surrounding the bilateral kidneys, and thickened mucous membrane of the bladder with high fluorodeoxyglucose uptake. Pathological examination of the pulmonary mass revealed infiltration of medium-sized lymphocytes and plasma cells. Immunohistochemical analysis revealed tumor cells positive for CD138 and IgM, with a low positive rate of Ki-67 expression. Notably, the tumor cell-surrounding lymphocytes were positive for CD20. Although the patient was initially regarded as having Waldenström's macroglobulinemia owing to the significantly increased serum IgM levels, based on positive IgH-MALT1 translocation and negative MYD88 L265P mutation findings, he was further diagnosed with extranodal marginal zone lymphoma of mucosa-associated lymphoid tissue (MALT lymphoma). Complete remission was achieved following six cycles of rituximab + CHOP therapy. This study data suggest that analysis of the MYD88 L265P mutation in tumor cells is suitable for accurately diagnosing hematopoietic malignancies with increased IgM monoclonal protein.
一名60岁的慢性丙型肝炎男性患者因常规体检发现总蛋白和血清IgM水平(9500mg/dl)显著升高而转诊至我院。血液检查显示血清IgM单克隆蛋白和血清可溶性白细胞介素-2受体(sIL2R)水平升高。计算机断层扫描和氟脱氧葡萄糖正电子发射断层扫描显示肺部肿块、双侧肾脏周围异常软组织肿块以及膀胱黏膜增厚伴氟脱氧葡萄糖摄取增加。肺部肿块的病理检查显示有中等大小淋巴细胞和浆细胞浸润。免疫组织化学分析显示肿瘤细胞CD138和IgM阳性,Ki-67表达阳性率低。值得注意的是,肿瘤细胞周围的淋巴细胞CD20阳性。尽管患者最初因血清IgM水平显著升高而被认为患有华氏巨球蛋白血症,但基于IgH-MALT1易位阳性和MYD88 L265P突变阴性的结果,他被进一步诊断为黏膜相关淋巴组织结外边缘区淋巴瘤(MALT淋巴瘤)。利妥昔单抗+CHOP方案治疗六个周期后实现了完全缓解。本研究数据表明,分析肿瘤细胞中的MYD88 L265P突变适用于准确诊断IgM单克隆蛋白升高的造血系统恶性肿瘤。