Whitwell Jennifer L, Stevens Chase A, Duffy Joseph R, Clark Heather M, Machulda Mary M, Strand Edythe A, Martin Peter R, Utianski Rene L, Botha Hugo, Spychalla Anthony J, Senjem Matthew L, Schwarz Christopher G, Jack Clifford R, Ali Farwa, Hassan Anhar, Josephs Keith A
Department of Radiology Mayo Clinic Rochester Minnesota.
Department of Neurology Mayo Clinic Rochester Minnesota.
Mov Disord Clin Pract. 2019 May 29;6(6):452-461. doi: 10.1002/mdc3.12796. eCollection 2019 Jul.
The Movement Disorder Society clinical criteria for progressive supranuclear palsy (PSP) provide a framework for assessing the presence/severity of clinical symptoms and define a speech/language variant of PSP.
To evaluate the clinical criteria in a cohort of speech/language patients with longitudinal follow-up.
A total of 52 patients presenting with progressive apraxia of speech and/or agrammatic aphasia were followed longitudinally for up to 6 visits with clinical assessments and magnetic resonance imaging. We assessed oculomotor, postural instability, and akinesia diagnostic levels and determined whether patients met criteria for possible PSP-speech/language or probable PSP at each visit. Kaplan-Meier curves assessed time-to-event probabilities according to age. Statistical parametric mapping and midbrain volume were assessed according to disease progression.
Few PSP symptoms were observed early in the disease, with oculomotor abnormalities and falls first observed 2 years after onset. Falls were more common than vertical supranuclear gaze palsy. Bradykinesia and rigidity commonly developed but axial was rarely greater than appendicular rigidity. During follow-up, 54% met criteria for possible PSP-speech/language, 38% for probable PSP-Richardson's syndrome, and 38% for probable PSP-parkinsonism, most commonly 6 to 6.9 years after onset. The probability of developing PSP was greater when onset was at an age older than 70 years. Patients who progressed to probable PSP had more parkinsonism and oculomotor impairment at baseline and greater midbrain atrophy when compared with those who did not develop probable PSP.
Symptoms typical of PSP commonly develop in patients presenting with a progressive speech/language disorder. Older age appears to be an important prognostic factor in these patients.
运动障碍协会关于进行性核上性麻痹(PSP)的临床标准为评估临床症状的存在/严重程度提供了框架,并定义了PSP的言语/语言变体。
对一组有言语/语言症状的患者进行纵向随访,以评估这些临床标准。
对52例表现为进行性言语失用和/或语法性失语的患者进行了纵向随访,最多进行6次临床评估和磁共振成像检查。我们评估了动眼神经、姿势不稳和运动不能的诊断水平,并确定患者在每次随访时是否符合可能的PSP-言语/语言型或很可能的PSP标准。采用Kaplan-Meier曲线根据年龄评估事件发生时间概率。根据疾病进展情况评估统计参数映射和中脑体积。
疾病早期很少观察到PSP症状,动眼神经异常和跌倒首次出现在发病后2年。跌倒比垂直性核上性凝视麻痹更常见。运动迟缓及强直普遍出现,但轴性强直很少超过肢体强直。随访期间,54%的患者符合可能的PSP-言语/语言型标准,38%符合很可能的PSP-理查森综合征标准,38%符合很可能的PSP-帕金森型标准,大多数情况是在发病后6至6.9年。发病年龄大于70岁时发生PSP的概率更高。与未发展为很可能的PSP的患者相比,进展为很可能的PSP的患者在基线时帕金森症状和动眼神经损害更多,中脑萎缩更严重。
PSP的典型症状常见于表现为进行性言语/语言障碍的患者。年龄较大似乎是这些患者的一个重要预后因素。