Kawasaki Yuki, Ejiri Soichi, Hakozaki Michiyuki, Konno Shinichi
Department of Orthopaedic Surgery, Fukushima Medical University School of Medicine, Fukushima, Japan.
Department of Regional Medical Support for Orthopaedic Surgery, Fukushima Medical University School of Medicine, Fukushima, Japan.
J Hand Surg Asian Pac Vol. 2019 Sep;24(3):383-385. doi: 10.1142/S2424835519720160.
Idiopathic intrinsic contracture (IIC) with no history of trauma, ischemia, or spasticity is extremely rare. We report herein a case of impaired extension of the digits due to bilateral IICs occurred in a 30-year-old woman with a past medical history of eating disorder and amenorrhea. Although no previous case has been reported in the literature, eight similar cases of IIC have been presented at Japanese domestic conferences. In these eight cases and the present case, resection of the thenar muscle cords and unilateral resection of the lateral band were effective. Since IIC in patients with an eating disorder is a rare condition, it would be treated conservatively at first as tendon sheath inflammation or locking. However, this condition may be resistant to conservative treatment, and surgical treatment should be considered in such cases.
无创伤、缺血或痉挛病史的特发性内在肌挛缩（IIC）极为罕见。我们在此报告一例30岁女性因双侧IIC导致手指伸展障碍的病例，该患者既往有饮食失调和闭经病史。虽然此前文献中未报道过类似病例，但在日本国内会议上已展示了8例类似的IIC病例。在这8例病例以及本病例中，切除鱼际肌索和单侧切除外侧束均有效。由于饮食失调患者的IIC是一种罕见病症，起初可能会作为腱鞘炎或绞锁进行保守治疗。然而，这种病症可能对保守治疗有抵抗性，在这种情况下应考虑手术治疗。
