Sengul Demet, Sengul Ilker, Ozen Ozkan
Ann Ital Chir. 2019 Sep 19;90:S2239253X19030895.
Presenting an extraordinary case of Eagle's syndrome (ES) with the classical and follicular variant of papillary thyroid microcarcinoma (PTmC) and an uncommon stylohyoid ligament calsification, aside from O'Carroll's System.
A 52-year-old Turkish man with an histopathology of the follicular variant of PTmC (FVPTmC) of his right lobe and conventional PTmC of his left lobe of the thyroid with an adjuvant 100 mCi radioactive iodine (RAI) ablation was admitted. On the routine follow-up of the present case, a lineer structure at the 3rd compartment of neck in his ultrasonography, a styloid ligament calsification in his noncontrast computed tomography (CT), and a left styloid process of the temporal bone of 29 mm in size in his three-dimensional (3D) CT scanning had been revealed. Conclusively, an ES, Langlais Type III with The Calcification Pattern IV, was recognized.
A noninvasive peroral medical management was administered as a first-line treatment for the neuropathic sequelae of ES and it has provided relief of signs and symptoms without any recurrence to date, for three years and three months.
To our knowledge, it is an highly extreme and first case of ES in the English literature, recognized in the course of his programmed follow-up of his conventional PTmC and FVPTmC, simultaneously possessing an exceptional stylohyoid ligament calsification, apart from O'Carroll's System, even with an anatomic variation of the hyoid bone.
Eagle's Syndrome Follicular variant of papillary thyroid microcarcinoma, Hyoid bone variation, Langlais classification, O'Carroll's System, Radioactive iodine, Papillary thyroid microcarcinoma.
除了奥卡罗尔系统外,报告一例罕见的鹰综合征(ES)病例,该病例伴有经典型和滤泡型甲状腺微小乳头状癌(PTmC)以及罕见的茎突舌骨韧带钙化。
一名52岁的土耳其男性因右叶甲状腺滤泡型PTmC(FVPTmC)和左叶传统PTmC的组织病理学检查结果入院,并接受了100毫居里放射性碘(RAI)辅助消融治疗。在该病例的常规随访中,超声检查发现颈部第三区有一条线性结构,非增强计算机断层扫描(CT)显示茎突舌骨韧带钙化,三维(3D)CT扫描显示颞骨左侧茎突长度为29毫米。最终,确诊为ES,朗格莱三世型伴钙化模式IV型。
对ES的神经病变后遗症采用无创经口药物治疗作为一线治疗方法,迄今为止,在三年零三个月的时间里,症状和体征得到缓解,且无任何复发。
据我们所知,这是英文文献中极为罕见的首例ES病例,在对其传统PTmC和FVPTmC进行定期随访过程中被发现,除了奥卡罗尔系统外,同时还伴有罕见的茎突舌骨韧带钙化,甚至舌骨存在解剖变异。
鹰综合征;甲状腺微小乳头状癌滤泡型;舌骨变异;朗格莱分类;奥卡罗尔系统;放射性碘;甲状腺微小乳头状癌