Agrawal Saurav Shishir, Mishra Chandan Kumar, Agrawal Chhavi, Chakraborty Partha Pratim
Endocrinology and Metabolism, Medical College and Hospital Kolkata, Kolkata, West Bengal, India.
Endocrinology and Metabolism, Medical College and Hospital Kolkata, Kolkata, West Bengal, India
BMJ Case Rep. 2020 Jan 21;13(1):e233350. doi: 10.1136/bcr-2019-233350.
Rickets other than those associated with advanced kidney disease, isolated distal renal tubular acidosis (dRTA) and hypophosphatasia (defective tissue non-specific alkaline phosphatase) are associated with hypophosphatemia due to abnormal proximal tubular reabsorption of phosphate. dRTA, however, at times is associated with completely reversible proximal tubular dysfunction. On the other hand, severe hypophosphatemia of different aetiologies may also interfere with both distal tubular acid excretion and proximal tubular functions giving rise to transient secondary renal tubular acidosis (distal and/or proximal). Hypophosphatemia and non-anion gap metabolic acidosis thus pose a diagnostic challenge occasionally. A definitive diagnosis and an appropriate management of the primary defect results in complete reversal of the secondary abnormality. A child with vitamin D resistant rickets was thoroughly evaluated and found to have primary dRTA with secondary proximal tubular dysfunction in the form of phosphaturia and low molecular weight proteinuria. The child was treated only with oral potassium citrate. A complete clinical, biochemical and radiological improvement was noticed in follow-up.
除了与晚期肾病、孤立性远端肾小管酸中毒(dRTA)和低磷血症(组织非特异性碱性磷酸酶缺陷)相关的佝偻病外,其他佝偻病与由于近端肾小管对磷酸盐重吸收异常导致的低磷血症有关。然而,dRTA有时与完全可逆的近端肾小管功能障碍有关。另一方面,不同病因的严重低磷血症也可能干扰远端肾小管酸排泄和近端肾小管功能,导致短暂的继发性肾小管酸中毒(远端和/或近端)。因此,低磷血症和非阴离子间隙代谢性酸中毒偶尔会带来诊断挑战。对原发性缺陷进行明确诊断并进行适当治疗可使继发性异常完全逆转。对一名维生素D抵抗性佝偻病患儿进行了全面评估,发现其患有原发性dRTA,并伴有继发性近端肾小管功能障碍,表现为磷酸盐尿和低分子量蛋白尿。该患儿仅接受口服柠檬酸钾治疗。随访中发现临床、生化和影像学均有完全改善。