Division of Clinical Medicine, Department of Nephrology, Faculty of Medicine, University of Tsukuba, 1-1-1 Tennoudai, Tsukuba, Ibaraki, 305-8575, Japan.
CEN Case Rep. 2020 Nov;9(4):354-358. doi: 10.1007/s13730-020-00482-w. Epub 2020 May 9.
an 80-year-old woman presented with rapidly progressive glomerulonephritis and was admitted to our hospital. Myeloperoxidase-specific antineutrophil cytoplasmic antibody (MPO-ANCA) was positive. We diagnosed ANCA-associated renal vasculitis (ANCA-RV). Treatment was initiated with intravenous methylprednisolone pulse therapy, followed by prednisolone (PSL) at 30 mg/day. We gradually reduced the PSL dose to 7.5 mg/day over 6 months. At that time, the patient developed disturbances of consciousness which progressed subacutely. MRI revealed regions of patchy white matter with an increased signal on T2-weighted, fluid attenuated inversion recovery (FLAIR) sequences and diffusion-weighted sequences. JC virus DNA was detected in the cerebrospinal fluid (CSF) by polymerase chain reaction (PCR), leading to a diagnosis of progressive multifocal leukoencephalopathy (PML). PML is a rare infectious demyelinating disease of the central nervous system caused by JC virus infection, occurring in highly immunosuppressed individuals such as HIV-infected patients and patients using some biological agents, and having a very poor prognosis. In the present case, PML may have been associated with steroid use, although there are very few case reports of PML in patients taking only steroids. We report progressive multifocal leukoencephalopathy during steroid treatment of ANCA-RV. When patients show progressive disturbance of consciousness during treatment for ANCA-RV, we need to take PML into consideration for differential diagnosis.
一位 80 岁女性因进行性肾小球肾炎入院。髓过氧化物酶特异性抗中性粒细胞胞质抗体(MPO-ANCA)阳性。我们诊断为 ANCA 相关性血管炎(ANCA-RV)。治疗开始时采用静脉注射甲基泼尼松龙脉冲治疗,随后给予泼尼松龙(PSL)30mg/天。我们在 6 个月内逐渐将 PSL 剂量减少至 7.5mg/天。此时,患者出现意识障碍,并逐渐加重。MRI 显示片状脑白质,T2 加权像、液体衰减反转恢复(FLAIR)序列和弥散加权序列信号增强。聚合酶链反应(PCR)检测到脑脊液(CSF)中 JC 病毒 DNA,从而诊断为进行性多灶性白质脑病(PML)。PML 是一种由 JC 病毒感染引起的中枢神经系统罕见的传染性脱髓鞘疾病,发生在高度免疫抑制的个体,如 HIV 感染者和使用某些生物制剂的患者,预后非常差。在本例中,PML 可能与类固醇的使用有关,尽管在仅使用类固醇的患者中,PML 的病例报告非常少。我们报告了在治疗 ANCA-RV 期间类固醇治疗引起的进行性多灶性白质脑病。当患者在接受 ANCA-RV 治疗时出现进行性意识障碍,我们需要考虑 PML 进行鉴别诊断。