Avalle Lidia, Marino Francesca, Camporeale Annalisa, Guglielmi Chiara, Viavattene Daniele, Bandini Silvio, Conti Laura, Cimino James, Forni Marco, Zanini Cristina, Ghigo Alessandra, Bogorad Roman L, Cavallo Federica, Provero Paolo, Koteliansky Victor, Poli Valeria
Department of Molecular Biotechnology and Health Science, University of Torino, Via Nizza 52, Torino 10126, Italy.
EuroClone S.p.A Research Laboratory, Molecular Biotechnology Center, University of Turin, Torino 10126, Italy.
Mol Ther Methods Clin Dev. 2020 May 22;18:62-72. doi: 10.1016/j.omtm.2020.05.023. eCollection 2020 Sep 11.
Myocarditis can lead to autoimmune disease, dilated cardiomyopathy, and heart failure, which is modeled in the mouse by cardiac myosin immunization (experimental autoimmune myocarditis [EAM]). Signal transducer and activator of transcription 3 (STAT3) systemic inhibition exerts both preventive and therapeutic effects in EAM, and STAT3 constitutive activation elicits immune-mediated myocarditis dependent on complement C3 and correlating with activation of the STAT3-interleukin 6 (IL-6) axis in the liver. Thus, liver-specific STAT3 inhibition may represent a therapeutic option, allowing to bypass the heart toxicity, predicted by systemic STAT3 inhibition. We therefore decided to explore the effectiveness of silencing liver Stat3 and C3 in preventing EAM onset and/or the recovery of cardiac functions. We first show that complement C3 and C5 genetic depletion significantly prevents the onset of spontaneous myocarditis, supporting the complement cascade as a viable target. In order to interfere with complement production and STAT3 activity specifically in the liver, we took advantage of liver-specific Stat3 or C3 small interfering (si)RNA nanoparticles, demonstrating that both siRNAs can significantly prevent myocarditis onset and improve the recovery of heart functions in EAM. Our data demonstrate that liver-specific Stat3/C3 siRNAs may represent a therapeutic option for autoimmune myocarditis and suggest that complement levels and activation might be predictive of progression to dilated cardiomyopathy.
心肌炎可导致自身免疫性疾病、扩张型心肌病和心力衰竭,在小鼠中可通过心肌肌球蛋白免疫(实验性自身免疫性心肌炎 [EAM])来模拟。信号转导和转录激活因子 3(STAT3)的全身抑制在 EAM 中具有预防和治疗作用,而 STAT3 的组成性激活会引发依赖补体 C3 且与肝脏中 STAT3 - 白细胞介素 6(IL - 6)轴激活相关的免疫介导性心肌炎。因此,肝脏特异性 STAT3 抑制可能是一种治疗选择,可避免全身 STAT3 抑制所预测的心脏毒性。我们因此决定探索沉默肝脏 Stat3 和 C3 在预防 EAM 发病和/或心脏功能恢复方面的有效性。我们首先表明,补体 C3 和 C5 的基因缺失可显著预防自发性心肌炎的发生,支持补体级联反应作为一个可行的靶点。为了特异性干扰肝脏中的补体产生和 STAT3 活性,我们利用了肝脏特异性 Stat3 或 C3 小干扰(si)RNA 纳米颗粒,证明这两种 siRNA 均可显著预防心肌炎的发生并改善 EAM 中心脏功能的恢复。我们的数据表明,肝脏特异性 Stat3/C3 siRNA 可能是自身免疫性心肌炎的一种治疗选择,并提示补体水平和激活可能预示着向扩张型心肌病的进展。