Medical Research Council Integrative Epidemiology Unit, Population Health Sciences, University of Bristol, Bristol, UK.
Institute of Cardiovascular Science, University College London, London, UK.
Genet Epidemiol. 2020 Nov;44(8):924-933. doi: 10.1002/gepi.22343. Epub 2020 Jul 24.
It has been hypothesised that nonsyndromic cleft lip/palate (nsCL/P) and cancer may share aetiological risk factors. Population studies have found inconsistent evidence for increased incidence of cancer in nsCL/P cases, but several genes (e.g., CDH1, AXIN2) have been implicated in the aetiologies of both phenotypes. We aimed to evaluate shared genetic aetiology between nsCL/P and oral cavity/oropharyngeal cancers (OC/OPC), which affect similar anatomical regions. Using a primary sample of 5,048 OC/OPC cases and 5,450 controls of European ancestry and a replication sample of 750 cases and 336,319 controls from UK Biobank, we estimate genetic overlap using nsCL/P polygenic risk scores (PRS) with Mendelian randomization analyses performed to evaluate potential causal mechanisms. In the primary sample, we found strong evidence for an association between a nsCL/P PRS and increased odds of OC/OPC (per standard deviation increase in score, odds ratio [OR]: 1.09; 95% confidence interval [CI]: 1.04, 1.13; p = .000053). Although confidence intervals overlapped with the primary estimate, we did not find confirmatory evidence of an association between the PRS and OC/OPC in UK Biobank (OR 1.02; 95% CI: 0.95, 1.10; p = .55). Mendelian randomization analyses provided evidence that major nsCL/P risk variants are unlikely to influence OC/OPC. Our findings suggest possible shared genetic influences on nsCL/P and OC/OPC.
人们假设非综合征性唇裂/腭裂(nsCL/P)和癌症可能具有共同的病因风险因素。人群研究发现,nsCL/P 病例的癌症发病率增加的证据不一致,但有几个基因(例如 CDH1、AXIN2)被认为与这两种表型的病因有关。我们旨在评估 nsCL/P 和口腔/口咽癌(OC/OPC)之间的遗传病因是否具有共同性,因为它们影响相似的解剖区域。使用欧洲血统的 5048 例 OC/OPC 病例和 5450 例对照的原始样本和来自 UK Biobank 的 750 例病例和 336319 例对照的复制样本,我们使用 nsCL/P 多基因风险评分(PRS)进行遗传重叠估计,并进行孟德尔随机化分析以评估潜在的因果机制。在原始样本中,我们发现 nsCL/P PRS 与 OC/OPC 患病风险增加之间存在很强的关联(评分每增加一个标准差,比值比 [OR]:1.09;95%置信区间 [CI]:1.04,1.13;p=0.000053)。尽管置信区间与主要估计值重叠,但我们在 UK Biobank 中没有发现 PRS 与 OC/OPC 之间关联的确认证据(OR 1.02;95% CI:0.95,1.10;p=0.55)。孟德尔随机化分析提供了证据表明,主要的 nsCL/P 风险变异不太可能影响 OC/OPC。我们的研究结果表明,nsCL/P 和 OC/OPC 可能具有共同的遗传影响。