• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利：CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法，用中文像聊天一样搜索，搜遍4000万医学文献。AI智能推荐，让科研检索更轻松。

立即免费搜索

文件翻译

保留排版，准确专业，支持PDF/Word/PPT等文件格式，支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述，25分钟生成高质量综述，智能提取关键信息，辅助科研写作。

立即免费体验

低体重新生儿先天性肠闭锁合并肠系膜囊性淋巴管瘤：一例报告

Congenital intestinal atresia associated with a mesenteric cystic lymphangioma in a low birth weight neonate: A case report.

作者信息

Fukuta Atsuhisa, Inoue Takayuki, Kawakubo Naonori, Kondo Takaya, Matsuura Toshiharu

机构信息

Department of Pediatric Surgery, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan; Department of Pediatric Surgery, Saga-Ken Medical Center Koseikan, Saga, Japan.

Department of Pediatric Surgery, Saga-Ken Medical Center Koseikan, Saga, Japan.

出版信息

Int J Surg Case Rep. 2020;75:136-139. doi: 10.1016/j.ijscr.2020.09.021. Epub 2020 Sep 10.

DOI:10.1016/j.ijscr.2020.09.021
PMID:32949911
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC7502782/
Abstract

INTRODUCTION

Congenital intestinal atresia requires emergency surgery soon after birth. Lymphangioma, a benign tumor, is caused by an anomalous lymphatic system. We report a case of congenital intestinal atresia associated with a mesenteric cystic lymphangioma in a low birth weight neonate.

PRESENTATION OF CASE

At 21 weeks of pregnancy, ultrasonography revealed a cystic lesion in the fetal abdominal cavity. At 31 weeks, magnetic resonance imaging showed dilatation of the small intestine. This low birth weight (1752 g) male infant was born by vaginal delivery at 32 weeks 3 days' gestation. Laparotomy on day 2 of life revealed jejunal atresia and a mesenteric cyst. The cyst was removed and intestinal anastomosis was performed. Histologically, the cyst proved to be a mesenteric lymphangioma.

DISCUSSION

The most popular theories regarding the mechanism of congenital intestinal atresia include reperfusion injury and intestinal tract blood flow disturbance. In this fetus, intestinal torsion had occurred around the mesenteric cystic lymphangioma, which apparently disturbed the mesenteric blood flow and caused intestinal atresia.

CONCLUSION

There have been few reports of the combination of a mesenteric cystic lymphangioma and congenital intestinal atresia. This case supports the theory that small bowel atresia and stenosis are caused by accidental blood flow disturbance.

摘要

引言

先天性肠闭锁出生后需尽快进行急诊手术。淋巴管瘤是一种良性肿瘤，由异常的淋巴系统引起。我们报告一例低体重新生儿先天性肠闭锁合并肠系膜囊性淋巴管瘤的病例。

病例介绍

妊娠21周时，超声检查发现胎儿腹腔有一囊性病变。31周时，磁共振成像显示小肠扩张。这名低体重（1752克）男婴在孕32周3天时经阴道分娩出生。出生后第2天进行剖腹手术，发现空肠闭锁和一个肠系膜囊肿。切除囊肿并进行了肠吻合术。组织学检查证实该囊肿为肠系膜淋巴管瘤。

讨论

关于先天性肠闭锁机制的最流行理论包括再灌注损伤和肠道血流紊乱。在这个胎儿中，围绕肠系膜囊性淋巴管瘤发生了肠扭转，这显然扰乱了肠系膜血流并导致肠闭锁。

结论

肠系膜囊性淋巴管瘤与先天性肠闭锁合并的报道很少。该病例支持小肠闭锁和狭窄是由意外的血流紊乱引起的这一理论。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/d4aa98ffed31/gr4.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/5237bb791646/gr1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/a66d7adcacf3/gr2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/43bcb2d1fb68/gr3.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/d4aa98ffed31/gr4.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/5237bb791646/gr1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/a66d7adcacf3/gr2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/43bcb2d1fb68/gr3.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/291e/7502782/d4aa98ffed31/gr4.jpg

相似文献

1
Congenital intestinal atresia associated with a mesenteric cystic lymphangioma in a low birth weight neonate: A case report.低体重新生儿先天性肠闭锁合并肠系膜囊性淋巴管瘤：一例报告
Int J Surg Case Rep. 2020;75:136-139. doi: 10.1016/j.ijscr.2020.09.021. Epub 2020 Sep 10.
2
Jejunal mesenteric lymphangioma treated by pancreaticoduodenectomy: A case report.胰十二指肠切除术治疗空肠系膜淋巴管瘤：一例报告。
Int J Surg Case Rep. 2020;77:165-169. doi: 10.1016/j.ijscr.2020.10.088. Epub 2020 Oct 22.
3
Small bowel volvulus and mesenteric ischemia induced by mesenteric cystic lymphangioma in an adult and literature review; a case report.成人肠系膜囊性淋巴管瘤致小肠扭转及肠系膜缺血并文献复习：一例报告
Int J Surg Case Rep. 2023 Apr;105:108083. doi: 10.1016/j.ijscr.2023.108083. Epub 2023 Mar 30.
4
Mesenteric cystic lymphangioma: a congenital and an acquired anomaly? Two cases and a review of the literature.肠系膜囊性淋巴管瘤：先天性和后天性异常？两例病例及文献综述
J Pediatr Surg. 2008 Jun;43(6):1206-8. doi: 10.1016/j.jpedsurg.2008.01.075.
5
[Mesenteric cysts].[肠系膜囊肿]
Acta Med Croatica. 2002;56(3):119-24.
6
Ileal volvulus secondary to cystic lymphangioma: A rare case report with a literature review.继发于囊性淋巴管瘤的回肠扭转：1例罕见病例报告并文献复习
Avicenna J Med. 2019 Apr-Jun;9(2):82-85. doi: 10.4103/ajm.AJM_203_18.
7
Mesenteric cystic lymphangioma associated with intestinal malrotation in a newborn.
Pediatr Med Chir. 2011 May-Jun;33(3):141-2.
8
Rupture of a giant jejunal mesenteric cystic lymphangioma misdiagnosed as ovarian torsion: A case report.误诊为卵巢扭转的巨大空肠系膜囊性淋巴管瘤破裂：一例报告
World J Clin Cases. 2024 Feb 6;12(4):847-852. doi: 10.12998/wjcc.v12.i4.847.
9
Mesenteric cystic lymphangioma misdiagnosed as ovarian cyst in a 63-year-old female: A case report and review of literature.一名63岁女性肠系膜囊性淋巴管瘤误诊为卵巢囊肿：病例报告及文献复习
Int J Surg Case Rep. 2024 Jul;120:109846. doi: 10.1016/j.ijscr.2024.109846. Epub 2024 Jun 1.
10
Prenatal ultrasonographic diagnosis of abdominal cystic lymphangioma: a case report.
J Matern Fetal Neonatal Med. 2008 Aug;21(8):565-6. doi: 10.1080/14767050802165927.

引用本文的文献

1
Management outcomes of mesenteric cysts in paediatric age group.小儿肠系膜囊肿的治疗结果。
Afr J Paediatr Surg. 2022 Jan-Mar;19(1):32-35. doi: 10.4103/ajps.AJPS_158_20.

本文引用的文献

1
The SCARE 2018 statement: Updating consensus Surgical CAse REport (SCARE) guidelines.SCARE 2018 声明：更新共识手术病例报告（SCARE）指南。
Int J Surg. 2018 Dec;60:132-136. doi: 10.1016/j.ijsu.2018.10.028. Epub 2018 Oct 18.
2
A histopathological diagnosis of mesenteric cystic lymphangioma, clinically misdiagnosed as simple mesenteric cyst - case report.肠系膜囊性淋巴管瘤的组织病理学诊断，临床误诊为单纯肠系膜囊肿——病例报告
Rom J Morphol Embryol. 2017;58(4):1525-1530.
3
Enlarging cystic lymphangioma of the mediastinum in an adult: is this a neoplastic lesion related to the recently discovered PIK3CA mutation?
成人纵隔巨大囊性淋巴管瘤：这是一种与最近发现的PIK3CA突变相关的肿瘤性病变吗？
Int J Clin Exp Pathol. 2015 May 1;8(5):5924-8. eCollection 2015.
4
Lymphatic and other vascular malformative/overgrowth disorders are caused by somatic mutations in PIK3CA.淋巴管及其他血管畸形/过度生长疾病由PIK3CA基因的体细胞突变引起。
J Pediatr. 2015 Apr;166(4):1048-54.e1-5. doi: 10.1016/j.jpeds.2014.12.069. Epub 2015 Feb 11.
5
Lymphangioma of the small bowel mesentery: a case report and review of the literature.小肠系膜淋巴管瘤：病例报告及文献复习。
World J Gastroenterol. 2012 Nov 21;18(43):6328-32. doi: 10.3748/wjg.v18.i43.6328.
6
Giant cystic lymphangioma of the mesentery: varied clinical presentation of 3 cases.肠系膜巨大囊性淋巴管瘤：3例的不同临床表现
Pan Afr Med J. 2012;12:7. Epub 2012 May 12.
7
PI3K signalling: the path to discovery and understanding.PI3K 信号通路：探索与理解之路。
Nat Rev Mol Cell Biol. 2012 Feb 23;13(3):195-203. doi: 10.1038/nrm3290.
8
Comparative outcomes in intestinal atresia: a clinical outcome and pathophysiology analysis.肠闭锁的比较结果：临床结局与病理生理学分析
Pediatr Surg Int. 2011 Apr;27(4):437-42. doi: 10.1007/s00383-010-2729-8. Epub 2010 Sep 4.
9
Congenital intestinal atresia; observations on its origin.先天性肠闭锁；关于其起源的观察
Lancet. 1955 Nov 19;269(6899):1065-7. doi: 10.1016/s0140-6736(55)92852-x.
10
The association of jejunal atresia and cystic lymphangioma in the same location.
J Pediatr Surg. 2003 Aug;38(8):1255-7. doi: 10.1016/s0022-3468(03)00283-5.