Myrianthopoulos N C, Melnick M
Am J Med Genet. 1987 Apr;26(4):783-96. doi: 10.1002/ajmg.1320260405.
In the NIH Collaborative Perinatal Project, a prospective study of over 53,000 pregnant women and their offspring, 71 single-born children (13.33/10,000) were found to have a non-syndromal neural tube defect (NTD). A family history was present in only one case. The group of individuals with NTD was compared to a group of 400 randomly selected non-malformed control infants. Of over 50 maternal factors studied the following showed significant association with NTD in the offspring: diabetes mellitus; organic heart disease; lung disease; and diuretic, antihistamine, and sulfonamide use. The interval between the termination of the immediately previous pregnancy and the start of the proband pregnancy was significantly shorter in mothers of NTD children than in mothers of control infants. The risk for NTD was also significantly increased if the immediately previous pregnancy was a spontaneous abortion. There was no increased risk for NTDs among sibs of children with major malformations such as tracheo-esophageal "dysraphism," cleft lip/palate, or renal agenesis. NTDs are apparently etiologically heterogeneous.
在美国国立卫生研究院围产期协作项目中,一项针对53000多名孕妇及其后代的前瞻性研究发现,71名单胎出生儿童(每10000例中有13.33例)患有非综合征性神经管缺陷(NTD)。仅有1例有家族病史。将患有NTD的个体组与400名随机选择的无畸形对照婴儿组进行比较。在研究的50多种母亲因素中,以下因素与后代的NTD有显著关联:糖尿病;器质性心脏病;肺部疾病;以及使用利尿剂、抗组胺药和磺胺类药物。NTD儿童的母亲中,上一次妊娠结束至先证者妊娠开始的间隔时间明显短于对照婴儿的母亲。如果上一次妊娠是自然流产,NTD的风险也会显著增加。患有诸如气管食管“闭合不全”、唇腭裂或肾发育不全等重大畸形的儿童的同胞中,NTD的风险没有增加。NTD显然在病因上具有异质性。